Burt Anna L, Daly Maureen P, Sherman Janet C, Schmahmann Jeremy D
Ataxia Center, Laboratory for Neuroanatomy and Cerebellar Neurobiology, Division of Behavioral Neurology & Integrated Brain Health, Department of Neurology, Mass General Brigham and Harvard Medical School, MGH Ataxia Center, 101 Merrimac Street, Suite 310, Boston, MA, 02114, USA.
Mesulam Center for Cognitive Neurology and Alzheimer's Disease, Northwestern University Feinberg School of Medicine, Chicago, IL, USA.
Cerebellum. 2025 May 5;24(4):94. doi: 10.1007/s12311-025-01840-z.
There is currently no established screening instrument that detects neuropsychiatric features in individuals with cerebellar ataxia. We hypothesized that the Cerebellar Neuropsychiatric Rating Scale (CNRS) would capture the neuropsychiatry of patients enrolled in the natural history study of the Clinical Research Consortium for the Study of Cerebellar Ataxia, and provide novel insights not revealed by other measures. We studied CNRS data in 362 patients with spinocerebellar ataxia types 1, 2, 3, 6, 7, 8, 10, and 27B, and cerebellar ataxia, neuropathy, vestibular areflexia syndrome (CANVAS). We grouped patients by mild, moderate, and severe disease severity according to Friedreich Ataxia Rating Scale (FARS) functional stage. We analyzed scores on the CNRS and its five constituent domains for the entire cohort and by severity subgroup. We fit a mixed effects model to examine the effect of severity. We analyzed correlations with other clinical measures: Cerebellar Cognitive Affective / Schmahmann Syndrome Scale (CCAS-S), Patient-Reported Outcome Measure of Ataxia (PROM-Ataxia), Patient Health Questionnaire-9 (PHQ-9), Euro-Qol 5-Dimension (EQ-5D), and Fatigue Severity Scale (FSS). The CNRS detected neuropsychiatric symptoms, with highest scores on Attentional and Emotional Control domains. The mixed effects model revealed that ataxia severity influences scores, with mean scores increasing with ataxia severity. The CNRS correlated with the PROM-Ataxia Mental domain, particularly between Emotional Control and section 1 (psychiatric) items. Emotional Control also correlated with PHQ-9 and EQ-5D. Correlations with the CCAS-S Affect and FSS were weak. The CNRS provides novel neuropsychiatric insights into spinocerebellar ataxia that are missed by other measures.
目前尚无既定的筛查工具可检测小脑共济失调患者的神经精神特征。我们假设小脑神经精神评定量表(CNRS)能够捕捉参与小脑共济失调临床研究联盟自然史研究的患者的神经精神状况,并提供其他测量方法未揭示的新见解。我们研究了362例1型、2型、3型、6型、7型、8型、10型和27B型脊髓小脑共济失调患者以及小脑共济失调、神经病变、前庭无反射综合征(CANVAS)患者的CNRS数据。我们根据弗里德赖希共济失调评定量表(FARS)功能阶段,将患者按轻度、中度和重度疾病严重程度进行分组。我们分析了整个队列以及严重程度亚组的CNRS及其五个组成领域的得分。我们拟合了一个混合效应模型来检验严重程度的影响。我们分析了与其他临床测量指标的相关性:小脑认知情感/施马曼综合征量表(CCAS-S)、患者报告的共济失调结局测量指标(PROM-共济失调)、患者健康问卷-9(PHQ-9)、欧洲五维健康量表(EQ-5D)和疲劳严重程度量表(FSS)。CNRS检测到了神经精神症状,注意力和情绪控制领域得分最高。混合效应模型显示,共济失调严重程度会影响得分,平均得分随共济失调严重程度增加而升高。CNRS与PROM-共济失调心理领域相关,尤其是情绪控制与第1部分(精神)项目之间。情绪控制也与PHQ-9和EQ-5D相关。与CCAS-S情感和FSS的相关性较弱。CNRS为脊髓小脑共济失调提供了其他测量方法未发现的新的神经精神见解。