Vietri Maria Teresa, Della Pepa Chiara, Caliendo Gemma, Mignano Alessia, Albanese Luisa, Zitiello Marialaura, Stilo Marianna, Molinari Anna Maria
Department of Precision Medicine, University of Campania "Luigi Vanvitelli", S. Andrea delle Dame, Via L. De Crecchio, 7, 80138 Napoli, Italy.
Unit of Clinical and Molecular Pathology, AOU University of Campania "Luigi Vanvitelli", S. Andrea delle Dame, Via L. De Crecchio, 7, 80138 Napoli, Italy.
Int J Mol Sci. 2025 Jun 20;26(13):5928. doi: 10.3390/ijms26135928.
Hereditary breast and ovarian cancer (HBOC) syndrome is primarily associated with mutations in BRCA1 and BRCA2, but increasing evidence links it to other malignancies, including male breast, prostate, and pancreatic cancers. Advances in genetic testing have led to the use of multigene panels, revealing that additional genes contribute to HBOC risk. We tested 280 patients with suspected HBOC using a multigene panel including BRCA1, BRCA2, and other genes involved in homologous recombination (HR) and additional DNA repair mechanisms. Variants were classified as pathogenic variants (PVs), variants of uncertain significance (VUS), or novel. In silico tools were used to predict the clinical relevance of VUS and novel variants. The clinical phenotype of families carrying a PV was evaluated. PVs were identified in 19.3% of patients: 8.9% in BRCA1/2 and 10.4% in other genes, mainly CHEK2, ATM, PALB2, and BRIP1. An additional 1.8% of cases harbored likely pathogenic VUS or novel variants according to bioinformatic prediction. Breast and ovarian cancer were the most frequent malignancies in our population, both in the BRCA group and in those with PVs in other susceptibility genes. Broad genetic testing beyond BRCA improves HBOC diagnostics, supports identification of at-risk families, and enables more personalized surveillance and treatment.
遗传性乳腺癌和卵巢癌(HBOC)综合征主要与BRCA1和BRCA2基因突变相关,但越来越多的证据表明它与其他恶性肿瘤有关,包括男性乳腺癌、前列腺癌和胰腺癌。基因检测技术的进步促使了多基因检测板的使用,结果显示其他基因也会增加HBOC风险。我们使用包含BRCA1、BRCA2以及其他参与同源重组(HR)和其他DNA修复机制的基因的多基因检测板,对280例疑似HBOC患者进行了检测。变异被分类为致病性变异(PV)、意义未明的变异(VUS)或新变异。利用计算机工具预测VUS和新变异的临床相关性。对携带PV的家系的临床表型进行了评估。在19.3%的患者中鉴定出PV:BRCA1/2基因中占8.9%,其他基因中占10.4%,主要是CHEK2、ATM、PALB2和BRIP1。根据生物信息学预测,另有1.8%的病例携带可能致病的VUS或新变异。乳腺癌和卵巢癌是我们研究人群中最常见的恶性肿瘤,在BRCA组和其他易感基因携带PV的患者中都是如此。除BRCA基因外进行广泛的基因检测可改善HBOC的诊断,有助于识别高危家系,并实现更个性化的监测和治疗。