Berke Gergő, Sahin-Tóth Miklós
Department of Surgery, University of California Los Angeles, Los Angeles, CA, 90095, USA.
Department of Surgery, University of California Los Angeles, 675 Charles E Young Drive South, MRL 2220, Los Angeles, CA, 90095, USA.
Sci Rep. 2025 Aug 2;15(1):28222. doi: 10.1038/s41598-025-13128-7.
The digestive enzyme trypsin is an important driver of pancreatitis development and progression. Inhibition of intrapancreatic trypsin activity is an attractive yet so far unsuccessful approach for the treatment and prevention of pancreatitis. Gene therapy using adeno-associated viral vector containing the human serine protease inhibitor Kazal type 1 (SPINK1) gene has shown efficacy against murine pancreatitis in preclinical experiments. To advance this method to clinical testing, viral vectors with improved inhibitor expression are needed. In this study, we investigated the effect of minigenes with single introns on the expression of the mouse Spink1 gene. We found that minigenes markedly stimulated the expression of mouse Spink1 mRNA and SPINK1 protein in HEK 293T cells transfected with plasmids and in AR42J rat pancreatic acinar cells and isolated mouse pancreatic acini transduced with adenoviral vectors. The optimal intron size for expression enhancement was 100 nucleotides. We also demonstrated that mouse Spink1 mRNA expressed from a cDNA construct underwent spurious mRNA splicing and minigenes prevented this splicing defect. However, enhancement of mouse Spink1 expression by minigenes was unrelated to the rescue of aberrant mRNA splicing. The observations will facilitate the development of advanced viral vectors harboring mouse Spink1 for preclinical therapeutic studies in mouse models of pancreatitis.
消化酶胰蛋白酶是胰腺炎发生和发展的重要驱动因素。抑制胰腺内胰蛋白酶活性是治疗和预防胰腺炎的一种有吸引力但迄今未成功的方法。使用含有人类丝氨酸蛋白酶抑制剂Kazal 1型(SPINK1)基因的腺相关病毒载体进行基因治疗已在临床前实验中显示出对小鼠胰腺炎的疗效。为了将这种方法推进到临床试验,需要具有改善抑制剂表达的病毒载体。在本研究中,我们研究了带有单个内含子的小基因对小鼠Spink1基因表达的影响。我们发现,小基因在转染质粒的HEK 293T细胞、AR42J大鼠胰腺腺泡细胞以及用腺病毒载体转导的分离小鼠胰腺腺泡中显著刺激了小鼠Spink1 mRNA和SPINK1蛋白的表达。增强表达的最佳内含子大小为100个核苷酸。我们还证明,从cDNA构建体表达的小鼠Spink1 mRNA发生了错误的mRNA剪接,而小基因可防止这种剪接缺陷。然而,小基因对小鼠Spink1表达的增强与异常mRNA剪接的挽救无关。这些观察结果将有助于开发携带小鼠Spink1的先进病毒载体,用于胰腺炎小鼠模型的临床前治疗研究。