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线粒体疾病合并局灶节段性肾小球硬化的视网膜多模态成像及功能测试

Retinal multimodal-imaging and functional tests in a mitochondrial disease with focal and segmental glomerulosclerosis.

作者信息

Liu Xiao-Hong, Shen Xi, Zhong Yi-Sheng

机构信息

Department of Ophthalmology, Ruijin Hospital, Shanghai Jiao Tong University School of Medicine, Shanghai 200025, China.

出版信息

Int J Ophthalmol. 2025 Sep 18;18(9):1770-1776. doi: 10.18240/ijo.2025.09.19. eCollection 2025.

Abstract

The phenotypes of the adenine-to-guanine transition at position 3243 of mitochondrial DNA (m.3243A>G) are highly variable, with different symptoms observed in different patients. These include mitochondrial encephalomyopathy, lactic acidosis, and stroke-like episodes (MELAS); maternally inherited diabetes and deafness syndrome (MIDD); other syndromic conditions; or non-syndromic mitochondrial disorders. Renal involvement associated with this mutation generally manifests as subnephrotic proteinuria, progressive deterioration of kidney function, and increased morbidity. The retinopathies linked to the m.3243A>G mutation have heterogeneous presentations, characterized by variable degrees of retinal pigment epithelium (RPE) atrophy and hyperpigmentation at the posterior pole. As a severe phenotype of the m.3243A>G mutation, MELAS combined with focal and segmental glomerulosclerosis (FSGS) is rare. We herein firstly reported in detail the ophthalmic manifestations of a patient with this condition. Additionally, we reviewed the literature on fundus, ophthalmic electrophysiology, and optical coherence tomography (OCT) findings related to the m.3243A>G mutation.

摘要

线粒体DNA 3243位腺嘌呤到鸟嘌呤的转换(m.3243A>G)的表型高度可变,不同患者表现出不同症状。这些症状包括线粒体脑肌病、乳酸酸中毒和卒中样发作(MELAS);母系遗传糖尿病和耳聋综合征(MIDD);其他综合征性疾病;或非综合征性线粒体疾病。与该突变相关的肾脏受累通常表现为亚肾病性蛋白尿、肾功能进行性恶化和发病率增加。与m.3243A>G突变相关的视网膜病变表现多样,其特征是后极部视网膜色素上皮(RPE)萎缩和色素沉着程度各异。作为m.3243A>G突变的一种严重表型,MELAS合并局灶节段性肾小球硬化(FSGS)较为罕见。我们在此首次详细报告了一名患有这种疾病的患者的眼部表现。此外,我们还回顾了有关m.3243A>G突变的眼底、眼科电生理学和光学相干断层扫描(OCT)检查结果的文献。

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