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妊娠合并先天性肌无力综合征:一例报告及围产期管理策略的文献综述

Congenital Myasthenic Syndrome in Pregnancy: A Case Report and Literature Review on Peripartum Management Strategy.

作者信息

Gnanarathne Sampath, Ratnayake Ashani, Thennewatte Dilum, Isurindi U A

机构信息

Department of Obstetrics and Gynaecology, Faculty of Medicine, University of Peradeniya, Kandy, LKA.

Department of Anaesthesiology and Critical Care, Faculty of Medicine, University of Peradeniya, Kandy, LKA.

出版信息

Cureus. 2025 Aug 4;17(8):e89337. doi: 10.7759/cureus.89337. eCollection 2025 Aug.

Abstract

Congenital myasthenic syndromes (CMS) are a group of rare inherited neuromuscular disorders caused by defects in neuromuscular transmission. Unlike autoimmune myasthenia gravis, CMS typically presents in childhood with variable severity and symptoms, and does not involve autoantibodies. This report presents the management of a primigravida diagnosed with CMS who was generally stable on pyridostigmine therapy but experienced a severe exacerbation during pregnancy. The diagnosis of CMS was made on clinical grounds, but the genetic testing for confirmation of the exact mutation was not available. The patient experienced intermittent mild exacerbations before pregnancy, managed with short courses of prednisolone. A severe exacerbation at 20 weeks of gestation required intensive care unit admission for respiratory support. Despite plans for a vaginal delivery, she developed exhaustion and desaturation during labour, followed by foetal distress, necessitating emergency caesarean section. Postpartum, the patient returned to her baseline functional status, and the neonate showed no signs of neuromuscular weakness. This case highlights that pregnancy in women with CMS can be safely managed with careful monitoring, multidisciplinary planning, and readiness to escalate care when needed. Delivery plans should be flexible, and management should be tailored to the individual's clinical course. Since the neonatal outcome is unpredictable in the absence of genetic testing, follow-up care is necessary in all cases.

摘要

先天性肌无力综合征(CMS)是一组由神经肌肉传递缺陷引起的罕见遗传性神经肌肉疾病。与自身免疫性重症肌无力不同,CMS通常在儿童期出现,严重程度和症状各不相同,且不涉及自身抗体。本报告介绍了一名初产妇的治疗情况,该产妇被诊断为CMS,在接受吡啶斯的明治疗时总体病情稳定,但在怀孕期间病情严重加重。CMS的诊断基于临床依据,但当时无法进行基因检测以确认确切的突变情况。该患者在怀孕前经历了间歇性轻度加重,通过短期使用泼尼松龙进行治疗。妊娠20周时病情严重加重,需要入住重症监护病房进行呼吸支持。尽管计划进行阴道分娩,但她在分娩过程中出现疲惫和血氧饱和度下降,随后出现胎儿窘迫,因此需要紧急剖宫产。产后,患者恢复到基线功能状态,新生儿未出现神经肌肉无力的迹象。该病例表明,对于患有CMS的女性,通过仔细监测、多学科规划以及在需要时随时加强护理,可以安全地管理妊娠。分娩计划应灵活多变,管理应根据个体的临床病程进行调整。由于在没有基因检测的情况下新生儿结局不可预测,因此所有病例都需要进行随访护理。

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