Sugimoto T, Matsumura T, Sakamoto Y, Taniuchi K
Brain Dev. 1979;1(4):323-6. doi: 10.1016/s0387-7604(79)80049-2.
A 5-year-old Japanese male with intractable running and laughing fits was reported to have had status epilepticus from 18 hours after birth. This intractable convulsions were thought to be due to hyperviscosity syndrome induced by neonatal idiopathic polycythemia. A phlebotomy ended the convulsions in the neonatal period, but the EEG continued to display right temporal spikes afterwards. He suffered from running and laughing fits 3 to 5 times daily from the age of 2 years up to 4 years 8 months. EEG revealed generalized dysrhythmia and poly-spikes and waves, mainly in the right side. Computerized tomography showed dilatation of all the ventricles plus multiple low density areas in the right temporal lobe. This case of running and laughing fits was presumed to be one of the temporal lobe epilepsy induced by the hyperviscosity syndrome brought on by neonatal polycythemia.
据报道，一名5岁日本男性患有难治性奔跑和痴笑发作，自出生后18小时起就出现癫痫持续状态。这种难治性惊厥被认为是由新生儿特发性红细胞增多症引起的高黏滞综合征所致。新生儿期的一次放血治疗结束了惊厥，但之后脑电图仍显示右颞叶有尖波。从2岁到4岁8个月，他每天会出现3至5次奔跑和痴笑发作。脑电图显示广泛性节律紊乱以及多棘波和慢波，主要出现在右侧。计算机断层扫描显示所有脑室扩张，右颞叶有多个低密度区。这例奔跑和痴笑发作被推测是由新生儿红细胞增多症引发的高黏滞综合征所致的颞叶癫痫之一。
