Prévot J, Schmitt M, Vidailhet M
Prog Pediatr Surg. 1983;16:97-106.
Two cases of pheochromocytomas in multiple locations are described. In the first case, a 5-year-old girl had surgery for a pheochromocytoma that was nonsecreting but had obstructed the renal artery. Ten years later, hypertension recurred and 2 adrenal pheochromocytomas, one on the left and one on the right side, were discovered. In addition, a papillary angioma was present in the fundus of the right eye, which indicated a phacomatosis. The child was cured. In the second case, another 5-year-old girl had a secreting pheochromocytoma in the upper thoracic region. Six months after extirpation of the tumour, a second pheochromocytoma was found in the right adrenal gland. These findings indicate 4 points of interest: 1. The thoracic localization. This prompted a review of all the available literature with the conclusion that this form of tumour is extremely rare. 2. The association of a pheochromocytoma and renal arterial stenosis. This has been observed by a number of other authors as well. 3. The coincidence of a pheochromocytoma as part of a phacomatosis and pheochromocytomas associated with Sipple's syndrome. 4. The multiple tumour sites. The necessity of generalized examinations in patients with pheochromocytomas to determine the presence of a phacomatosis or Sipple's syndrome is apparent.
本文描述了两例多部位嗜铬细胞瘤病例。第一例,一名5岁女孩因非分泌性但阻塞肾动脉的嗜铬细胞瘤接受手术。十年后,高血压复发,发现双侧肾上腺嗜铬细胞瘤,左侧一个,右侧一个。此外,右眼眼底有一个乳头状血管瘤,提示存在错构瘤病。该患儿治愈。第二例,另一名5岁女孩在上胸部区域有一个分泌性嗜铬细胞瘤。肿瘤切除六个月后,在右侧肾上腺发现第二个嗜铬细胞瘤。这些发现提示了四个有趣的点:1. 胸部定位。这促使对所有现有文献进行回顾,得出这种肿瘤形式极为罕见的结论。2. 嗜铬细胞瘤与肾动脉狭窄的关联。其他一些作者也观察到了这一点。3. 嗜铬细胞瘤作为错构瘤病的一部分与与西普尔综合征相关的嗜铬细胞瘤同时存在。4. 多个肿瘤部位。对于嗜铬细胞瘤患者进行全面检查以确定是否存在错构瘤病或西普尔综合征的必要性显而易见。