Jeraj K, Kim Y, Vernier R L, Fish A J, Michael A F
Am J Kidney Dis. 1983 May;2(6):626-9. doi: 10.1016/s0272-6386(83)80043-2.
The presence of Goodpasture's (GP) antigen in the glomerular basement membrane (GBM) of the kidney was evaluated by indirect immunofluorescence in nine patients with familial nephritis from five kindreds. The GP antigen was not detected in seven males but was present in an affected sister and mother, an unaffected brother, and 13 normal controls. The specificity of this finding in affected males is supported by the persistence of other GBM antigens identified by monoclonal antibodies. The lack of GP antigen in affected males and its persistence in related females with the disease suggests a possible X-linked dominant mode of inheritance. We propose that the absence of GP antigen leads to severe disease in the male, whereas its presence in related females is associated with mild disease.
通过间接免疫荧光法对来自五个家族的九名家族性肾炎患者肾的肾小球基底膜(GBM)中Goodpasture(GP)抗原的存在情况进行了评估。在七名男性患者中未检测到GP抗原,但在一名患病姐妹和母亲、一名未患病兄弟以及13名正常对照中检测到了该抗原。单克隆抗体鉴定出的其他GBM抗原持续存在,支持了这一在患病男性中发现的特异性。患病男性中缺乏GP抗原,而在患病相关女性中持续存在,提示可能存在X连锁显性遗传模式。我们认为,GP抗原的缺失导致男性病情严重,而其在相关女性中的存在与病情较轻有关。