Preus M, Linstrom C, Polomeno R C, Milot J
Am J Med Genet. 1983 Jul;15(3):383-8. doi: 10.1002/ajmg.1320150303.
We have estimated that 83% of individuals carrying the gene for Waardenburg syndrome type I show penetrance of the gene as measured by dystopia canthorum. This is lower than previous estimates, which failed to consider the frequency of equivocal dystopia in the general population. The addition of three other major signs (hearing loss, white forelock, and premature graying of the hair or vitiligo) does not substantially increase the discrimination of gene carriers (85% versus 83%). We estimate that about 75% of the first-degree relatives of probands can be assigned as normal or a gene carrier on the basis of the four major signs.
我们估计,携带Ⅰ型瓦登伯格综合征基因的个体中,83%的人表现出该基因的外显率,这是通过内眦异位来衡量的。这一比例低于之前的估计,之前的估计没有考虑到普通人群中模棱两可的内眦异位频率。再加上其他三个主要体征(听力丧失、白色额发以及头发过早变白或白癜风),并不会显著提高对基因携带者的鉴别率(分别为85%和83%)。我们估计,根据这四个主要体征,先证者的一级亲属中约75%的人可被判定为正常或基因携带者。