Parry D M, Li F P, Strong L C, Carney J A, Schottenfeld D, Reimer R R, Grufferman S
J Natl Cancer Inst. 1982 Apr;68(4):573-8.
Genetic factors in the etiology of carotid body tumors (CBT) were sought in a medical record review of 222 histologically diagnosed cases at 12 U.S. medical centers. Patients in the series, which had a marked female predominance (146 females:76 males), usually developed tumors between the fourth and seventh decades of life (mean, 44.7 yr). In 16 patients who also had other extra-adrenal paragangliomas, suggesting a multiple primary tumor syndrome, CBT were diagnosed significantly earlier (mean, 35.4 yr; P less than 0.01). The occurrence of thyroid cancer in 5 other patients appeared to be excessive. Familial CBT was recognized in 16 patients from 13 affected families, including 9 newly ascertained kindreds. Compared with non-familial lesions, familial CBT tended to develop bilaterally (38% vs. 8% unilaterally) and at slightly earlier ages (41.6 vs. 44.9 yr). CBT was reported to occur in an autosomal dominant pattern in some families and within sibships in others; relatives were not examined for confirmation. The familial findings are generally consistent with a two-step mutation model of the development of hereditary and nonhereditary CBT; apparent deviations from the model might be clarified with additional data on this rare neoplasm.
在美国12家医疗中心对222例经组织学确诊的颈动脉体瘤(CBT)病例进行的病历回顾中,探寻了CBT病因中的遗传因素。该系列患者中女性明显居多(女性146例:男性76例),通常在40至70岁之间发病(平均44.7岁)。16例同时患有其他肾上腺外副神经节瘤的患者提示存在多原发性肿瘤综合征,其CBT诊断明显更早(平均35.4岁;P<0.01)。另外5例患者中甲状腺癌的发生似乎过多。在13个受累家庭的16例患者中识别出家族性CBT,包括9个新确诊的亲属关系。与非家族性病变相比,家族性CBT倾向于双侧发生(38%对单侧8%)且发病年龄稍早(41.6岁对44.9岁)。据报道,CBT在一些家族中呈常染色体显性模式发生,在其他家族中则在同胞中发生;未对亲属进行检查以证实。家族性研究结果总体上与遗传性和非遗传性CBT发生的两步突变模型一致;该罕见肿瘤的更多数据可能会澄清与该模型明显的偏差。