Kyong C U, Virella G, Fudenberg H H, Darby C P
Pediatr Res. 1978 Oct;12(10):1024-6. doi: 10.1203/00006450-197810000-00015.
Two cases of immunodeficiency with increased IgM are reported. Patient 1 was a black male 3.5 years old who had recurrent pyogenic infections, failure to thrive, oral thrush, and systemic cryptococcal infection. Patient 2 was a 9-year-old white female who had recurrent cervical abscesses. Serum immunoglobulin determinations by radial immunodiffusion in both patients showed marked depression of IgG and IgA and marked elevation of IgM. A low molecular weight circulating monomeric IgM was demonstrated by immunoelectrophoresis and gel filtration in the second patient; this was not present in the first case. In vitro impairment of cellular immunity was observed in both patients. Administration of dialyzable leukocyte extracts (transfer factor) led to improvement of cell-mediated immunity in patient 1. The etiology of this syndrome apparently has several different genetic bases. These patients demonstrate heterogeneity in genetic, ethnic, immunologic, and other features of the syndrome.
报告了两例伴有IgM升高的免疫缺陷病例。病例1是一名3.5岁的黑人男性,有反复的化脓性感染、发育不良、口腔念珠菌病和全身性隐球菌感染。病例2是一名9岁的白人女性,有反复的颈部脓肿。通过放射免疫扩散法对两名患者进行血清免疫球蛋白测定,结果显示IgG和IgA显著降低,IgM显著升高。通过免疫电泳和凝胶过滤在第二名患者中证实存在低分子量循环单体IgM;第一例中不存在这种情况。两名患者均观察到细胞免疫的体外损伤。对病例1给予可透析白细胞提取物(转移因子)后,细胞介导的免疫功能得到改善。该综合征的病因显然有几种不同的遗传基础。这些患者在该综合征的遗传、种族、免疫和其他特征方面表现出异质性。