Nat Genet. 1995 Oct;11(2):130-6. doi: 10.1038/ng1095-130.
X-linked hypophosphatemic rickets (HYP) is a dominant disorder characterised by impaired phosphate uptake in the kidney, which is likely to be caused by abnormal regulation of sodium phosphate cotransport in the proximal tubules. By positional cloning, we have isolated a candidate gene from the HYP region in Xp22.1. This gene exhibits homology to a family of endopeptidase genes, members of which are involved in the degradation or activation of a variety of peptide hormones. This gene (which we have called PEX) is composed of multiple exons which span at least five cosmids. Intragenic non-overlapping deletions from four different families and three mutations (two splice sites and one frameshift) have been detected in HYP patients, which suggest that the PEX gene is involved in the HYP disorder.
X连锁低磷性佝偻病(HYP)是一种显性疾病,其特征是肾脏对磷酸盐的摄取受损,这可能是由近端小管中钠磷协同转运的异常调节引起的。通过定位克隆,我们从Xp22.1的HYP区域分离出一个候选基因。该基因与一个内肽酶基因家族具有同源性,该家族成员参与多种肽激素的降解或激活。这个基因(我们称之为PEX)由多个外显子组成,这些外显子跨越至少五个黏粒。在HYP患者中检测到来自四个不同家族的基因内非重叠缺失和三个突变(两个剪接位点和一个移码突变),这表明PEX基因与HYP疾病有关。