Komiyama A, Morosawa H, Nakahata T, Miyagawa Y, Akabane T
J Pediatr. 1979 Jan;94(1):19-25. doi: 10.1016/s0022-3476(79)80343-1.
Neutrophils from a patient with recurrent pyogenic infections since infancy were found to have morphologic abnormalities and impaired functions. The neutrophils had an abnormal nuclear shape, no or few secondary granules, and no alkaline phosphatase activity. Primary granules were normal in number and structure, and were positive for peroxidase. Immature granulocytes were structurally normal. The neutrophils were impaired in chemotaxis and bactericidal capacity. The patient's marrow cells formed increased numbers of granulocytic colonies of small size in culture. Her peripheral leukocytes produced elevated levels of CSA and adherent marrow cells did not inhibit colony formation. These data indicate an intrinsic neutrophil defect which allows normal proliferation of precursor cells, but results in abnormal morphogenesis and impaired function as the cells mature.
自婴儿期起就患有复发性化脓性感染的一名患者的中性粒细胞被发现存在形态异常和功能受损的情况。这些中性粒细胞具有异常的核形状,没有或仅有少量的次级颗粒,且没有碱性磷酸酶活性。初级颗粒在数量和结构上正常,且过氧化物酶呈阳性。未成熟粒细胞在结构上正常。这些中性粒细胞的趋化性和杀菌能力受损。该患者的骨髓细胞在培养中形成的粒细胞集落数量增加且体积小。她外周血白细胞产生的CSA水平升高,并且贴壁骨髓细胞不抑制集落形成。这些数据表明存在一种内在的中性粒细胞缺陷,它允许前体细胞正常增殖,但在细胞成熟时导致异常的形态发生和功能受损。