Johnstone H, Benirschke K
Obstet Gynecol. 1976 May;47(5):610-4.
This report describes premature monozygotic twins, 1 of whom had an unusual clinical manifestation of a rare congenital anomaly, the other being normally developed. Hydramnios had been suspected during pregnancy and, because of the severity, amniocentesis was attempted. However, it became evident that the hugely distended abdomen did not indicate hydramnios, the pregnancy actually being complicated by oligohydramnios. Pulmonary hypoplasia was the cause of the immediate neonatal demise of 1 twin; the other expired after prolonged therapy for meconium aspiration. No similar cases have been reported in the literature which is reviewed briefly. Particular attention is given to discordant anomalies in monozygotic twins, the mode of their placentation, and the development of amnion nodosum.
本报告描述了一对早产单卵双胞胎，其中一人出现了一种罕见先天性异常的不寻常临床表现，另一人发育正常。孕期曾怀疑有羊水过多，鉴于病情严重，尝试进行了羊膜穿刺术。然而，明显可见极度膨胀的腹部并非羊水过多所致，实际上该妊娠合并的是羊水过少。肺发育不全是其中一个双胞胎新生儿期立即死亡的原因；另一个在接受胎粪吸入的长期治疗后死亡。本文简要回顾了相关文献，未见有类似病例报道。特别关注了单卵双胞胎中的不一致性异常、其胎盘形成方式以及羊膜结节的发育情况。
