Migita M, Fukunaga Y, Ueda T, Watanabe A, Morita T, Yamamoto M
Department of Pediatrics, Nippon Medical School, Japan.
Nihon Ika Daigaku Zasshi. 1994 Nov;61(6):633-7. doi: 10.1272/jnms1923.61.633.
Gaucher disease is the most prevalent lysosomal storage disease. Although the efficacy of the macrophage-targeted human placental glucocerebrosidase is well known, it is still difficult to develop definitive guidelines regarding the appropriate therapy schedule. We describe an 8-year-old Japanese boy with Gaucher disease who had avascular necrosis of the right femoral head without deterioration of hematological variables during low-dose enzyme replacement therapy (12-13 IU/kg). This case demonstrates that continuous normal hematological findings may not preclude progression of other aspects of Gaucher disease in some patients during enzyme replacement therapy.
戈谢病是最常见的溶酶体贮积病。尽管巨噬细胞靶向的人胎盘葡萄糖脑苷脂酶的疗效已为人熟知,但制定关于适当治疗方案的明确指南仍很困难。我们描述了一名8岁的日本戈谢病男孩,他在低剂量酶替代治疗(12 - 13 IU/kg)期间出现了右侧股骨头缺血性坏死,而血液学指标并未恶化。该病例表明,在酶替代治疗期间,持续正常的血液学检查结果在某些患者中可能并不排除戈谢病其他方面的进展。