Lin D, Sugawara T, Strauss J F, Clark B J, Stocco D M, Saenger P, Rogol A, Miller W L
Department of Pediatrics, University of California, San Francisco 94143.
Science. 1995 Mar 24;267(5205):1828-31. doi: 10.1126/science.7892608.
Congenital lipoid adrenal hyperplasia is an autosomal recessive disorder that is characterized by impaired synthesis of all adrenal and gonadal steroid hormones. In three unrelated individuals with this disorder, steroidogenic acute regulatory protein, which enhances the mitochondrial conversion of cholesterol into pregnenolone, was mutated and nonfunctional, providing genetic evidence that this protein is indispensable normal adrenal and gonadal steroidogenesis.
先天性类脂性肾上腺增生症是一种常染色体隐性疾病,其特征为所有肾上腺和性腺类固醇激素的合成受损。在三名患有该疾病的无亲缘关系个体中,增强线粒体将胆固醇转化为孕烯醇酮的类固醇生成急性调节蛋白发生突变且无功能,这为该蛋白在正常肾上腺和性腺类固醇生成中不可或缺提供了遗传学证据。