Marinoni J C, Boyd E, Sherman S, Schwartz C
Greenwood Genetic Center, SC 29646.
Hum Mol Genet. 1994 Aug;3(8):1355-7. doi: 10.1093/hmg/3.8.1355.
Ectrodactyly (split hand/split foot, SHSF) is characterized by the absence of middle rays of the hand or the foot. Cytogenetic analyses of some of the cases have indicated an association between chromosomal rearrangements involving 7q21.3-q22 and ectrodactyly. Based on these observations, an autosomal dominant form of ectrodactyly is assumed to reside in this region and the locus has been designated SHFD1 (split hand/split foot disorder). Here we report a large family where split hand/split foot long bone deficiency (SHFLD) segregates in an autosomal dominant mode. Linkage analysis, using microsatellite markers located in 7q21-q22, excludes this region from containing the gene responsible for SHFLD in this family. These results would appear to indicate genetic heterogeneity exists in autosomal dominant SHSF.
缺指(趾)畸形(裂手/裂足,SHSF)的特征是手或足部中间指(趾)缺失。对部分病例的细胞遗传学分析表明,涉及7q21.3 - q22的染色体重排与缺指(趾)畸形有关。基于这些观察结果,假定缺指(趾)畸形的常染色体显性形式位于该区域,该基因座已被命名为SHFD1(裂手/裂足障碍)。在此,我们报告一个大家庭,其中裂手/裂足长骨发育不全(SHFLD)以常染色体显性模式分离。使用位于7q21 - q22的微卫星标记进行连锁分析,排除了该区域包含此家族中导致SHFLD的基因。这些结果似乎表明常染色体显性SHSF存在遗传异质性。