Aessopos A, Voskaridou E, Kavouklis E, Vassilopoulos G, Rombos Y, Gavriel L, Loukopoulos D
First Department of Medicine, Laiko General Hospital, Athens, Greece.
Am J Ophthalmol. 1994 May 15;117(5):589-92. doi: 10.1016/s0002-9394(14)70064-9.
Angioid streaks have been described in a diverse group of diseases including hemoglobinopathies such as sickle cell anemia and beta-thalassemia. We investigated the prevalence of angioid streaks and pseudoxanthoma elasticum in the rare situation of patients who had compound heterozygous traits for hemoglobin S and beta-thalassemia. We examined 58 consecutive patients with sickle-thalassemia. Of these, 25 were men and 33 were women, and they ranged in age from 19 to 58 years (mean, 32.6 years). Angioid streaks were identified in six of 58 patients (10%), and of these three also displayed the cutaneous lesions of pseudoxanthoma elasticum, which were confirmed by skin biopsy. An expanded study on several relatives of the patients with angioid streaks failed to identify any similar cases. Statistical evaluation of the main hematologic and biochemical parameters in the patients with and without angioid streaks did not demonstrate any significant differences, except that the thalassemic component in all six patients with angioid streaks was beta(0) (that is, did not allow the synthesis of hemoglobin A). We conclude that angioid streaks and pseudoxanthoma elasticum skin lesions occur with an increased frequency in patients with sickle-thalassemia.
血管样条纹已在多种疾病中被描述,包括血红蛋白病,如镰状细胞贫血和β地中海贫血。我们调查了患有血红蛋白S和β地中海贫血复合杂合性状的患者这一罕见情况下血管样条纹和弹性假黄瘤的患病率。我们检查了58例连续的镰状细胞贫血-地中海贫血患者。其中,25例为男性,33例为女性,年龄在19至58岁之间(平均32.6岁)。58例患者中有6例(10%)发现有血管样条纹,其中3例还表现出弹性假黄瘤的皮肤损害,经皮肤活检得以证实。对血管样条纹患者的几名亲属进行的扩大研究未发现任何类似病例。对有和没有血管样条纹的患者的主要血液学和生化参数进行统计评估,除了所有6例有血管样条纹的患者中的地中海贫血成分均为β0(即不允许合成血红蛋白A)外,未显示出任何显著差异。我们得出结论,血管样条纹和弹性假黄瘤皮肤损害在镰状细胞贫血-地中海贫血患者中出现的频率增加。