Prindiville D E, Stern D
J Oral Surg. 1976 Jul;34(7):603-8.
The oral lesions in two previously reported cases of fucosidosis are discussed. The patients have coarse facies, severe mental retardation, spondyloepiphyseal dysplasia, deficiency of a-L-fucosidase, and red punctate lesions of the skin and oral mucosa. Gingival biopsy specimens showed that these lesions were identical to the angiokeratoma corporis diffusum reported in Fabry's disease, but had different locations. Because of the slowly progressing psychomotor retardation and recurrent upper respiratory tract infections that the prognosis for patients with this disease is poor. Treatment appears to be aimed at early diagnosis through amniocentesis.
本文讨论了之前报道的两例岩藻糖苷贮积症患者的口腔病变。患者有粗糙面容、严重智力发育迟缓、脊椎骨骺发育不良、α-L-岩藻糖苷酶缺乏,以及皮肤和口腔黏膜的红色点状病变。牙龈活检标本显示,这些病变与法布里病中报道的弥漫性躯体血管角皮瘤相同,但位置不同。由于精神运动发育迟缓进展缓慢且反复发生上呼吸道感染,该疾病患者的预后较差。治疗似乎旨在通过羊膜穿刺术进行早期诊断。