Akinci A, Teziç T, Ertürk G, Tarim O, Dalva K
Pediatric Endocrinology Unit, Dr Sami Ulus Children's Hospital, Ankara, Turkey.
Acta Paediatr Jpn. 1993 Jun;35(3):262-6. doi: 10.1111/j.1442-200x.1993.tb03049.x.
This study introduces a patient who has thiamine and thiamine pyrophosphokinase (TPKase) enzyme deficiency associated with diabetes mellitus, sensorineural deafness and thiamine-responsive megaloblastic anemia. Diabetes mellitus was diagnosed when she was 20 months old. After 1 year, macrocytic anemia developed and the thiamine therapy was started at 75 mg/day. During the follow-up, the insulin requirement decreased and even ceased, and macrocytic anemia improved with thiamine treatment. After thiamine therapy was ceased an increase in insulin requirement was observed and macrocytic anemia developed again.
本研究介绍了一名患有硫胺素和硫胺素焦磷酸激酶(TPKase)酶缺乏症的患者,该病症与糖尿病、感音神经性耳聋和硫胺素反应性巨幼细胞贫血相关。她在20个月大时被诊断出患有糖尿病。1年后,出现了大细胞性贫血,并开始每天服用75毫克硫胺素进行治疗。在随访期间,胰岛素需求量减少甚至停止,硫胺素治疗使大细胞性贫血得到改善。停止硫胺素治疗后,观察到胰岛素需求量增加,大细胞性贫血再次出现。