Arenas-Sordo M de la L, Saavedra-Ontiveros D, Sánchez-Guerrero C, Torres-Carmona M A
Departamento de Genética, Hospital General Dr. Manuel Gea González, México, D. F.
Bol Med Hosp Infant Mex. 1993 Jan;50(1):48-52.
The Angelman syndrome or "happy puppet" syndrome is a disorder of severe mental retardation, seizure, paroxysms of laughter, absent speech, jerky movements and ataxic gait. We present two sibs, man and woman, with this disorder, fact that support the possible autosomal recessive inheritance as a cause of this pathology, which hereditary mechanism is still a controversial point. Besides, we can observe different expression, being the woman more severely affected than the man. To our knowledge, this is the first mexican family reported with this syndrome, and with a ten years follow up. Chromosomal studies, with high resolution technique, were normal, we did not find the 15 chromosomic deletion referred as a possible cause in some cases, that is why it is undeniable that genetic heterogeneity exists in this syndrome.
天使综合征或“快乐木偶”综合征是一种严重智力发育迟缓、癫痫发作、阵发性大笑、无语言能力、运动急促和共济失调步态的疾病。我们报告了一对患有这种疾病的同胞兄妹,一男一女,这一事实支持了常染色体隐性遗传可能是这种病症病因的观点,而其遗传机制仍是一个有争议的问题。此外,我们可以观察到不同的表现,女性比男性受影响更严重。据我们所知,这是首个报道的患有该综合征且随访十年的墨西哥家庭。采用高分辨率技术进行的染色体研究结果正常,我们未发现某些病例中提及的可能病因——15号染色体缺失,这就是为什么不可否认该综合征存在遗传异质性。