Takeshita M, Akamatsu M, Ohshima K, Kimura N, Suzumiya J, Kikuchi M, Okamura T, Nakayama J, Imayama S, Uike N
Department of Pathology, School of Medicine, Fukuoka University, Japan.
Hum Pathol. 1995 Dec;26(12):1321-8. doi: 10.1016/0046-8177(95)90296-1.
Eleven patients with angiocentric immunoproliferative lesion (AIL) of the skin were studied. Histologically, three patients were grouped into AIL grade II (AIL-II), whereas eight showed angiocentric lymphoma (AIL-III). All the patients' specimens exhibited lobular panniculitis. Infiltrating atypical lymphocytes in nine patients possessed electron-dense membrane bound granules in electron microscopy. Phenotypically, the lymphoid cells in the AIL-II patients were positive for CD3 epsilon; two of these showed a positive reaction to CD2, CD7, and CD8, but lacked natural killer-associated (NKa) antigens CD16, CD56, and CD57. In six AIL-III patients, lymphoma cells were positive for CD2 in all patients, CD56 in five, CD3 epsilon in four, CD7 in four, interleukin-2 beta receptor in four, a pore-forming protein in four, and CD30 in three patients. The remaining two AIL-III patients had B-cell lymphoma. By the Southern blot analysis, three patients with AIL-III showed a rearranged T-cell-receptor beta-gene or a deletion of its germline. The preceding results in nine of 11 patients suggest that abnormal or neoplastic large granular lymphocytes with the characteristics of T and NK cells have an important role in producing the angiocentric/angiodestructive features and lobular panniculitis. Clinically, all three patients with AIL-II and four with AIL-III showed liver dysfunction, cytopenia, and abnormal coagulopathy during the clinical course. Five patients with AIL-III died within 8 months. The histological grading of AIL, patients' age, and limited clinical stage of the disease seem to correlate with response to the treatment and prognosis.
对11例皮肤血管中心性免疫增殖性病变(AIL)患者进行了研究。组织学上,3例患者被归为AIL二级(AIL-II),而8例表现为血管中心性淋巴瘤(AIL-III)。所有患者的标本均表现为小叶性脂膜炎。9例患者的浸润性非典型淋巴细胞在电子显微镜下具有电子致密的膜结合颗粒。表型上,AIL-II患者的淋巴细胞对CD3ε呈阳性;其中2例对CD2、CD7和CD8呈阳性反应,但缺乏自然杀伤相关(NKa)抗原CD16、CD56和CD57。在6例AIL-III患者中,淋巴瘤细胞在所有患者中对CD2呈阳性,5例对CD56呈阳性,4例对CD3ε呈阳性,4例对CD7呈阳性,4例对白介素-2β受体呈阳性,4例对一种成孔蛋白呈阳性,3例对CD30呈阳性。其余2例AIL-III患者患有B细胞淋巴瘤。通过Southern印迹分析,3例AIL-III患者显示T细胞受体β基因重排或其种系缺失。11例患者中有9例的上述结果表明,具有T细胞和NK细胞特征的异常或肿瘤性大颗粒淋巴细胞在产生血管中心性/血管破坏性特征和小叶性脂膜炎方面起重要作用。临床上,3例AIL-II患者和4例AIL-III患者在临床过程中均出现肝功能障碍、血细胞减少和异常凝血病。5例AIL-III患者在8个月内死亡。AIL的组织学分级、患者年龄和疾病的临床分期似乎与治疗反应和预后相关。