Lacombe D, Pedespan J M, Fontan D, Chateil J F, Verloes A
Department of Medical Genetics, Pellegrin-Children's Hospital, University of Bordeaux II, France.
Genet Couns. 1995;6(3):221-6.
The association of lower lip pits with cleft lip and/or palate defines the van der Woude syndrome (VWS). VWS has an autosomal dominant mode of inheritance wiht a high penetrance and a variable expression. A gene involved in the origin of VWS is linked to loci on chromosome 1q32-q41. The gene might be involved in the programmed cell death of neural crest derived cells. Other malformations have been associated with the syndrome (dental defects, syngnathia, limb abnormalities, popliteal webs...). We report 4 cases with VWS demonstrating the wide clinical variability. One case shows brain abnormalities that might be part of the clinical spectrum of VWS.
下唇凹陷与唇裂和/或腭裂的关联定义了范德伍德综合征(VWS)。VWS具有常染色体显性遗传模式,具有高外显率和可变表达。一个与VWS起源相关的基因与1号染色体1q32 - q41上的位点相连。该基因可能参与神经嵴衍生细胞的程序性细胞死亡。其他畸形也与该综合征相关(牙齿缺陷、颌骨融合、肢体异常、腘窝蹼……)。我们报告了4例VWS病例,展示了其广泛的临床变异性。其中1例显示出脑部异常,这可能是VWS临床谱的一部分。