Battistella P A, Peserico A
Department of Pediatrics, University of Padua, Italy.
Childs Nerv Syst. 1996 Feb;12(2):110-3. doi: 10.1007/BF00819509.
This is a report of new case of PIBI(D)S, a rare autosomal recessive syndrome characterized by photosensitivity, ichthyosis, brittle sulfur-deficient hair (trichothiodystrophy), impaired intelligence, decreased fertility, and short stature. Bilateral cataract and axial osteosclerosis were also detected. Magnetic resonance imaging (MRI) revealed diffuse central nervous system dysmyelination, a finding also described in the only three other reported cases in which MRI was performed. The paper also considers certain similarities in neurological signs and neuroradiological findings between PIBI(D)S, Cockayne syndrome, and xeroderma pigmentosum--all of which are inherited diseases characterized by photosensitivity and DNA repair defect.
这是一篇关于PIBI(D)S新病例的报告,PIBI(D)S是一种罕见的常染色体隐性综合征,其特征为光敏性、鱼鳞病、硫缺乏性脆发(毛发硫营养不良)、智力受损、生育能力下降和身材矮小。还检测到双侧白内障和轴向骨硬化。磁共振成像(MRI)显示弥漫性中枢神经系统脱髓鞘,这一发现也在另外三例进行了MRI检查的报告病例中有所描述。本文还探讨了PIBI(D)S、科凯恩综合征和着色性干皮病在神经学体征和神经放射学检查结果方面的某些相似之处——所有这些都是以光敏性和DNA修复缺陷为特征的遗传性疾病。