Pausova Z, Soliman E, Amizuka N, Janicic N, Konrad E M, Arnold A, Goltzman D, Hendy G N
Department of Medicine, McGill University, Montreal, Quebec, Canada.
J Clin Endocrinol Metab. 1996 Jul;81(7):2711-8. doi: 10.1210/jcem.81.7.8675600.
Parathyroid tumors occur either sporadically or as part of inherited syndromes such as multiple endocrine neoplasia (MEN) types 2A and 2B. The development of both of these familial syndromes has been related to specific germline gain-of-function mutations predominantly in exons 10 and 11 (MEN 2A) and 16 (MEN 2B) of the RET proto-oncogene. The same mutations have also been implicated in the pathogenesis of sporadic medullary thyroid carcinoma and sporadic pheochromocytoma. The RET mutations are thought to have a transforming effect only in cells of neural crest origin such as thyroid parafollicular (C-cells) and adrenal chromaffin cells, which normally express the RET proto-oncogene. Expression of RET messenger RNA has not yet been studied in the parathyroid, however, we demonstrate in this study by a sensitive, semiquantitative RT-PCR technique and in situ hybridization, that RET is expressed in MEN 2A parathyroid tumors and in sporadic adenomas. Although DNA from a parathyroid tumor of a MEN 2A patient displayed an expected mutation, none of the previously described MEN 2A or 2B mutations were found in DNA of 34 sporadic adenomas. Our data suggest that parathyroid disease is an integral part of the MEN 2A syndrome, but that MEN 2 mutations in RET rarely play a part in the pathogenesis of sporadic parathyroid tumors.
甲状旁腺肿瘤可散发出现,也可作为遗传性综合征的一部分出现,如2A和2B型多发性内分泌腺瘤病(MEN)。这两种家族性综合征的发生都与RET原癌基因主要在外显子10和11(MEN 2A)以及16(MEN 2B)中的特定种系功能获得性突变有关。相同的突变也与散发性甲状腺髓样癌和散发性嗜铬细胞瘤的发病机制有关。RET突变被认为仅在神经嵴起源的细胞中具有转化作用,如甲状腺滤泡旁细胞(C细胞)和肾上腺嗜铬细胞,这些细胞通常表达RET原癌基因。甲状旁腺中尚未对RET信使核糖核酸的表达进行研究,然而,我们在本研究中通过灵敏的半定量逆转录聚合酶链反应技术和原位杂交证明,RET在MEN 2A甲状旁腺肿瘤和散发性腺瘤中表达。虽然一名MEN 2A患者的甲状旁腺肿瘤DNA显示出预期的突变,但在34例散发性腺瘤的DNA中未发现任何先前描述的MEN 2A或2B突变。我们的数据表明,甲状旁腺疾病是MEN 2A综合征的一个组成部分,但RET中的MEN 2突变很少在散发性甲状旁腺肿瘤的发病机制中起作用。