Park K C, Park S K, Lee Y S, Youn S W, Park B S, Kim K H, Lee S T
Department of Dermatology, Seoul National University College of Medicine, Korea.
Jpn J Hum Genet. 1996 Sep;41(3):299-305. doi: 10.1007/BF01913172.
Oculocutaneous albinism (OCA) is an inherited disorder of the melanin pigmentary system, characterized by a decrease or an absence of melanin in the skin, hair, and eyes. Type I (tyrosinase-deficient) OCA results from mutations of the tyrosinase (TYR) gene encoding tyrosinase, the enzyme that catalyzes at least the first two steps of melanin biosynthesis. We have analyzed the TYR gene in three Korean patients with severe type I OCA. Two patients were compound heterozygotes for the Arg (CGG) to Gln (CAG) mutation at position 77 and a C insertion mutation at position 310. The other was a compound heterozygote for a C insertion mutation at position 310 and the Asp (GAT) to Asn (AAT) mutation at position 383. These mutations were easily detected by restriction enzyme digestion or by SSCP analysis. Such methods of mutation analysis thus provide a basis for a screening system for the TYR gene mutations in Korean patients with type I OCA.
眼皮肤白化病(OCA)是一种遗传性黑色素色素系统疾病,其特征是皮肤、头发和眼睛中的黑色素减少或缺失。I型(酪氨酸酶缺乏型)OCA是由编码酪氨酸酶的酪氨酸酶(TYR)基因突变引起的,酪氨酸酶是催化黑色素生物合成至少前两步的酶。我们分析了三名患有严重I型OCA的韩国患者的TYR基因。两名患者是77位密码子由精氨酸(CGG)突变为谷氨酰胺(CAG)以及310位密码子发生C插入突变的复合杂合子。另一名患者是310位密码子C插入突变与383位密码子由天冬氨酸(GAT)突变为天冬酰胺(AAT)的复合杂合子。这些突变通过限制性内切酶消化或单链构象多态性(SSCP)分析很容易检测到。因此,这种突变分析方法为韩国I型OCA患者的TYR基因突变筛查系统提供了基础。