Suppr超能文献

皮质基底节变性:神经病理学与临床异质性

Corticobasal degeneration: neuropathologic and clinical heterogeneity.

作者信息

Schneider J A, Watts R L, Gearing M, Brewer R P, Mirra S S

机构信息

Veterans Affairs Medical Center, Decatur, GA 30033, USA.

出版信息

Neurology. 1997 Apr;48(4):959-69. doi: 10.1212/wnl.48.4.959.

Abstract

We investigated clinical and neuropathologic heterogeneity and apolipoprotein E (apoE) genotype in 11 cases of neuropathologically diagnosed corticobasal degeneration (CBD). Although seven of the 11 patients presented with unilateral limb dysfunction, the remaining four patients had less typical presentations including memory loss, behavioral changes, and difficulties with speech or gait. All 11 patients eventually developed extrapyramidal signs as well as cortical features, most commonly apraxia. At autopsy, the brains of seven of the 11 patients exhibited predominant neuronal loss and gliosis of perirolandic cortex; degeneration of more rostral frontal cortex was observed in three of the four patients with atypical clinical presentations. All cases displayed ballooned neurons, tau-positive neuronal and glial inclusions, threads and grains, and nigral degeneration. Six of the 11 cases manifested overlapping neuropathologic features of one or more disorders, including Alzheimer's disease (AD), progressive supranuclear palsy (PSP), Parkinson's disease (PD), and hippocampal sclerosis. Interestingly, these six patients all exhibited memory loss early in the course of their illness. The 11 CBD cases exhibited increased frequency (0.32) of the epsilon 4 allele of apoE, relative to control populations; the frequency remained elevated (0.25) even when the three cases with concomitant AD were excluded. Beta-amyloid (A beta) deposition in hippocampus or cortex was present in five of the seven cases with an epsilon 4 genotype. These observations indicate that CBD is a pathologically and clinically heterogeneous disorder with substantial overlap with other neurodegenerative disorders.

摘要

我们对11例经神经病理学诊断为皮质基底节变性(CBD)的患者进行了临床、神经病理学异质性及载脂蛋白E(apoE)基因型研究。虽然11例患者中有7例表现为单侧肢体功能障碍,但其余4例患者的临床表现不太典型,包括记忆力减退、行为改变以及言语或步态障碍。所有11例患者最终均出现锥体外系体征以及皮质特征,最常见的是失用症。尸检时,11例患者中有7例大脑表现为中央前回皮质的神经元大量丢失和胶质增生;4例临床表现不典型的患者中有3例观察到额叶皮质更靠前部位的变性。所有病例均显示有气球样神经元、tau阳性神经元和胶质包涵体、神经丝和颗粒以及黑质变性。11例病例中有6例表现出一种或多种疾病(包括阿尔茨海默病(AD)、进行性核上性麻痹(PSP)、帕金森病(PD)和海马硬化)重叠的神经病理学特征。有趣的是,这6例患者在病程早期均出现记忆力减退。与对照人群相比,11例CBD病例中apoE ε4等位基因的频率增加(0.32);即使排除3例合并AD的病例,该频率仍保持在较高水平(0.25)。在7例ε4基因型病例中有5例海马或皮质存在β淀粉样蛋白(Aβ)沉积。这些观察结果表明,CBD是一种在病理和临床上具有异质性的疾病,与其他神经退行性疾病有大量重叠。

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验