Khakoo A, Thomas R, Trompeter R, Duffy P, Price R, Pope F M
Department of Paediatrics, Northwick Park Hospital, Middlesex, UK.
Clin Genet. 1997 Feb;51(2):109-14. doi: 10.1111/j.1399-0004.1997.tb02430.x.
We report two phenotypically similar patients with primary cutis laxa associated with deficiency of lysyl oxidase, an extracellular copper enzyme the gene for which is located on chromosome 5. Previous reports of this condition have had characteristic occipital projections, abnormality of copper metabolism and X-linked inheritance. The two reported patients have no occipital projections, normal copper metabolism, Wormian bones, and a pattern of inheritance consistent with the autosomal recessive inheritance of the lysyl oxidase gene.
我们报告了两名表型相似的原发性皮肤松弛症患者,他们伴有赖氨酰氧化酶缺乏,这是一种细胞外铜酶,其基因位于5号染色体上。此前关于这种疾病的报道有特征性的枕部突出、铜代谢异常和X连锁遗传。而我们报告的这两名患者没有枕部突出,铜代谢正常,有缝间骨,其遗传模式与赖氨酰氧化酶基因的常染色体隐性遗传一致。