Rotman G, Shiloh Y
Department of Human Genetics, Sackler School of Medicine, Tel Aviv University, Ramat Aviv, Israel.
Bioessays. 1997 Oct;19(10):911-7. doi: 10.1002/bies.950191011.
Ataxia-telangiectasia (A-T) is a pleiotropic recessive disorder characterized by cerebellar ataxia, immunodeficiency, specific developmental defects, profound predisposition to cancer and acute radiosensitivity. Functional inactivation of a single gene product, ATM, accounts for this compound phenotype. We suggest that ATM acts as a sensor of reactive oxygen species and/or oxidative damage of cellular macromolecules, including DNA. In turn, ATM induces signalling through multiple pathways, thereby coordinating acute phase stress responses with cell cycle checkpoint control and repair of oxidative damage. Absence of ATM is proposed to limit the repair of insidious oxidative damage that can occur under normal physiological conditions, ultimately leading to apoptosis of particularly sensitive cells, such as neurons and thymocytes.
共济失调毛细血管扩张症(A-T)是一种多效性隐性疾病,其特征为小脑共济失调、免疫缺陷、特定发育缺陷、患癌倾向严重以及对辐射急性敏感。单一基因产物ATM的功能失活导致了这种复合表型。我们认为,ATM作为活性氧和/或包括DNA在内的细胞大分子氧化损伤的传感器。反过来,ATM通过多种途径诱导信号传导,从而协调急性期应激反应与细胞周期检查点控制以及氧化损伤修复。ATM的缺失被认为会限制在正常生理条件下可能发生的隐匿性氧化损伤的修复,最终导致特别敏感的细胞如神经元和胸腺细胞凋亡。