Wolkenstein P, Benchikhi H, Zeller J, Wechsler J, Revuz J
Department of Dermatology, Hôpital Henri-Mondor, Créteil, France. wolk@univ-paris 12.fr
Dermatology. 1997;195(3):228-31. doi: 10.1159/000245948.
Schwannomatosis includes multiple cutaneous schwannomas, central nervous system tumors and various neurologic deficits.
To specify the clinical presentation of schwannomatosis, excluding neurofibromatosis type 2 (NF2).
Patients with at least 2 cutaneous schwannomas were evaluated for NF2 criteria.
5 men and 2 women (mean age 54 +/- 18 years) we included. Two cases were familial. Cutaneous schwannomas were tender nodules with onset above the age of 30 years. Four patients had paresthesias. Four patients had hypacusis, but auditory brainstem responses showed no retrocochlear involvement. No vestibular schwannoma or central nervous system tumor was found with magnetic resonance imaging in 6 patients. Spinal imaging performed in 6 patients was normal in 5 and showed a spinal schwannoma in the 6th patient.
We strictly eliminated the diagnosis of NF2 in our patients. Exclusion of NF2 in suspected schwannomatosis is essential for further molecular genetic studies.
神经鞘瘤病包括多发性皮肤神经鞘瘤、中枢神经系统肿瘤及各种神经功能缺损。
明确神经鞘瘤病的临床表现,排除2型神经纤维瘤病(NF2)。
对至少有2个皮肤神经鞘瘤的患者进行NF2标准评估。
纳入5名男性和2名女性(平均年龄54±18岁)。2例为家族性。皮肤神经鞘瘤为压痛性结节,发病年龄在30岁以上。4例患者有感觉异常。4例患者有听力减退,但听觉脑干反应显示无蜗后受累。6例患者的磁共振成像未发现前庭神经鞘瘤或中枢神经系统肿瘤。6例患者进行的脊髓成像中,5例正常,第6例显示有脊髓神经鞘瘤。
我们在患者中严格排除了NF2的诊断。在疑似神经鞘瘤病中排除NF2对进一步的分子遗传学研究至关重要。