Frints S G, Schoenmakers E F, Smeets E, Petit P, Fryns J P
Center for Human Genetics, University Hospital Leuven, Belgium.
Am J Med Genet. 1998 Jan 13;75(2):153-8. doi: 10.1002/(sici)1096-8628(19980113)75:2<153::aid-ajmg6>3.0.co;2-u.
We report on a de novo 7q36 deletion in a 3-month-old girl with manifestations of the 7q terminal deletion syndrome. Only minimal findings of holoprosencephaly (HPE) were present since only a partial corpus callosum hypoplasia was seen on a magnetic resonance imaging scan of the brain. Extensive fluorescence in situ hybridization analysis showed that the HPE3 critical gene region, inclusive Sonic hedgehog (SHH), En2 (HOX1), and HTR5A, was deleted. A review of 33 other patients with a de novo terminal 7q deletion and the different types of HPE manifestations within these patients will be presented.
我们报告了一名3个月大患有7q末端缺失综合征表现的女孩的新发7q36缺失。由于在脑部磁共振成像扫描中仅发现部分胼胝体发育不全,所以仅存在全前脑畸形(HPE)的轻微表现。广泛的荧光原位杂交分析表明,HPE3关键基因区域,包括音猬因子(SHH)、En2(HOX1)和5-羟色胺受体5A(HTR5A)均被缺失。本文将对另外33例新发7q末端缺失患者以及这些患者中不同类型的HPE表现进行综述。