Funk M, Schmidt H, Escuriola-Ettingshausen C, Pons S, Dzinaj T, Weimer C, Kornhuber B, Kreuz W
Department of Pediatrics III, J.W. Goethe University, Frankfurt am Main, Germany.
Ann Hematol. 1998 Oct;77(4):171-4. doi: 10.1007/s002770050436.
In order to evaluate joint alteration, 17 patients with hemophilia A and B were investigated over a period of 4 years (1993-1997). Patients were subdivided into two groups, according to therapy regimens. In group 1 (n=10) prophylactic treatment was initiated until the third year of life. In group 2 (n=7) patients received prophylactic treatment at the age of 5 years and above. To assess alterations in knee, elbow, and ankle joints, the radiological score and the physical examination score of the Orthopedic Advisory Committee of the World Federation of Hemophilia were used. The sum of the scores of these six joints was defined as the patient-dependent score. Patients of group 1 (median age at the end of observation: 10 years) reached a median radiological score of 1.0 (range: 0-13) and an orthopedic score of 0 (range: 0-4), whereas patients of group 2 (median age: 14 years) had a radiological score of 20 (range: 2-47) and an orthopedic score of 8 (range: 0-12), which shows a significant difference (p <0.01). In both treatment groups a manifestation or progression of arthropathic alteration was seen in those children who had repeated joint bleeding (>5) prior to the onset of prophylactic treatment (r=0.90, p>0.01). Altogether, two of 60 joints in group 1 and 12 of 42 joints in group 2 had a radiological score > or = 4. Elbow joints were more often affected than knee and ankle joints. In conclusion, the number of joint bleedings before prophylactic treatment was started influenced the progression of arthropathy even in patients with early onset of prophylaxis. The aim of treatment in severe hemophilia should be early prophylaxis before repeated joint bleeding occurs in order to prevent osteoarthropathic alteration.
为了评估关节病变情况,对17例甲型和乙型血友病患者进行了为期4年(1993 - 1997年)的调查。根据治疗方案将患者分为两组。第1组(n = 10)从出生至3岁开始进行预防性治疗。第2组(n = 7)患者在5岁及以上开始接受预防性治疗。为评估膝关节、肘关节和踝关节的病变情况,采用了世界血友病联盟骨科咨询委员会的放射学评分和体格检查评分。这六个关节的评分总和被定义为患者相关评分。第1组患者(观察期末中位年龄:10岁)的放射学评分中位数为1.0(范围:0 - 13),骨科评分为0(范围:0 - 4),而第2组患者(中位年龄:14岁)的放射学评分为20(范围:2 - 47),骨科评分为8(范围:0 - 12),差异具有统计学意义(p <0.01)。在两个治疗组中,那些在预防性治疗开始前有反复关节出血(>5次)的儿童均出现了关节病性改变的表现或进展(r = 0.90,p>0.01)。总体而言,第1组60个关节中有2个、第2组42个关节中有12个的放射学评分≥4。肘关节比膝关节和踝关节更常受累。总之,即使对于早期开始预防的患者,预防性治疗开始前的关节出血次数也会影响关节病的进展。重度血友病的治疗目标应是在反复关节出血发生之前尽早进行预防,以防止骨关节病变。