Faro A
Pediatric Pulmonary Center, University of Florida, Gainesville 32610-0296, USA.
Springer Semin Immunopathol. 1998;20(3-4):425-36. doi: 10.1007/BF00838053.
EBV-transformation induces B lymphocytes to secrete high levels of human IL-10. Additionally, EBV contains a gene, BCRF1, that encodes for a protein that shares activity with human IL-10 in vitro. Thus, infection by EBV seems to promote a Th2 environment in the infected host. One may even hypothesize that EBV-derived IL-10 initiates a cascade of events that promotes a Th2 response and suppresses Th1 activity. This is further confirmed by data that suggest elevated concentrations of IL-4, IL-10, and IgE in patients with PTLD. This implies an association between PTLD and an imbalance in the immunoregulatory system with either an excess suppression of Th1 cells and/or an up-regulation of Th2 cells. One could speculate that if the imbalance in the immunoregulatory system is corrected, the patient's own immune system could potentially defend itself against the virus. Clearly, this is the case in those immunocompromised patients with PTLD who respond to just a reduction in their immunosuppression. Unfortunately, this is only beneficial in approximately half of patients with PTLD. Perhaps this is because patients often do not become entirely immunocompetent, either because all of their immunosuppression cannot be discontinued for fear of rejection or because once the above cascade is established the immune system is not capable of easily switching to the Th1 response necessary for combating the virus. Theoretically, IFN-alpha, because of its anti-viral effect, its anti-neoplastic effect and/or possibly by its ability to promote a Th1 response, should be useful in the treatment of PTLD. IFN-alpha modulates the immune system by several mechanisms including: preventing B cells from producing immunoglobulins, reducing IL-6 receptor density, and augmenting the inhibition of IL-4 by IL-12. In vitro studies document its effectiveness against EBV. Unfortunately, the available evidence as to its efficacy in vivo in patients with PTLD is very limited. At present, there are only 16 reported cases in the literature. There are also three cases of BLPD in immunocompromised patients that were all successfully treated with IFN-alpha and the two cases alluded to earlier from Children's Hospital of Pittsburgh (personal communication). Although the numbers are small, the results are promising. Of the 21 patients with BLPD who received IFN-alpha, 15 achieved complete remission. Four others improved and 2 died from BLPD. One of the 4 that improved died 3 months later from a relapse. Thus, there was an overall mortality of 14% (3 of 21) in those who received therapy with IFN-alpha. This is a very heterogeneous group of patients, several of whom had also received additional therapies. Thus, it is impossible to draw definitive conclusions. However, the mortality rate in this group of patients, who had already failed therapy with a reduction in their immunosuppression, compares very favorably to the reported mortality rate of approximately 23-81% in patients with PTLD. This data suggest that a large multi-centered prospective trial comparing IFN-alpha with and without IVIg to other treatment options (i.e., LAK cells) is warranted in those patients with EBV-positive PTLD who fail to respond to a reduction in their immunosuppression.
EB病毒转化可诱导B淋巴细胞分泌高水平的人白细胞介素-10。此外,EB病毒含有一个基因BCRF1,该基因编码一种在体外与人白细胞介素-10具有共同活性的蛋白质。因此,EB病毒感染似乎会在受感染宿主中促进Th2环境。甚至有人推测,EB病毒衍生的白细胞介素-10会引发一系列事件,促进Th2反应并抑制Th1活性。这一推测进一步得到了数据的证实,这些数据表明PTLD患者体内白细胞介素-4、白细胞介素-10和免疫球蛋白E的浓度升高。这意味着PTLD与免疫调节系统失衡之间存在关联,即Th1细胞过度受抑和/或Th2细胞上调。有人可能会推测,如果免疫调节系统的失衡得到纠正,患者自身的免疫系统可能有能力抵御病毒。显然,那些免疫功能低下的PTLD患者在免疫抑制降低后病情得到缓解,情况正是如此。不幸的是,这仅对约一半的PTLD患者有益。这可能是因为患者往往无法完全恢复免疫功能,要么是因为担心排斥反应而无法完全停止免疫抑制,要么是因为一旦上述级联反应建立,免疫系统就无法轻易转向对抗病毒所需的Th1反应。从理论上讲,α干扰素因其抗病毒作用、抗肿瘤作用和/或可能因其促进Th1反应的能力,应该对PTLD的治疗有用。α干扰素通过多种机制调节免疫系统,包括:阻止B细胞产生免疫球蛋白、降低白细胞介素-6受体密度以及增强白细胞介素-12对白细胞介素-4的抑制作用。体外研究证明了其对EB病毒的有效性。不幸的是,关于其在PTLD患者体内疗效的现有证据非常有限。目前,文献中仅报道了16例病例。免疫功能低下患者中还有3例BLPD病例,均成功接受了α干扰素治疗,以及前文提到的匹兹堡儿童医院的2例病例(个人交流)。尽管病例数量较少,但结果很有希望。在接受α干扰素治疗的21例BLPD患者中,15例完全缓解。另外4例病情改善,2例死于BLPD。4例病情改善的患者中有1例在3个月后因复发死亡。因此,接受α干扰素治疗的患者总死亡率为14%(21例中的3例)。这是一组非常异质的患者,其中一些人还接受了其他治疗。因此,无法得出明确结论。然而,这组已经接受免疫抑制降低治疗但治疗失败的患者的死亡率,与报道的PTLD患者约23%-81%的死亡率相比,要低得多。这些数据表明,对于EB病毒阳性的PTLD患者,在免疫抑制降低治疗无效的情况下,进行一项大型多中心前瞻性试验,比较α干扰素联合或不联合静脉注射免疫球蛋白与其他治疗方案(如淋巴因子激活的杀伤细胞)是有必要的。