Barbi G, Kennerknecht I, Wöhr G, Avramopoulos D, Karadima G, Petersen M B
Abteilung Medizinische Genetik der Universität, Ulm, Germany.
Am J Med Genet. 2000 Mar 13;91(2):116-22. doi: 10.1002/(sici)1096-8628(20000313)91:2<116::aid-ajmg7>3.0.co;2-q.
We report on a mentally retarded child with multiple minor anomalies and an unusually rearranged chromosome 21. This der(21) chromosome has a deletion of 21p and of proximal 21q, whereas the main portion of 21q is duplicated leading to a mirror-symmetric appearance with the mirror axis at the breakpoint. The centromere is only characterized by a secondary constriction (with a centromeric index of a G chromosome) at an unexpected distal position, but fluorescence in situ hybridization (FISH) with either chromosome specific or with all human centromeres alpha satellite DNA shows no cross hybridization. Thus, the marker chromosome represents a further example of an "analphoid marker with neocentromere." Molecular analysis using polymorphic markers on chromosome 21 verified a very small monosomic segment of the proximal long arm of chromosome 21, and additionally trisomy of the remaining distal segment. Although trisomic for almost the entire 21q arm, our patient shows no classical Down syndrome phenotype, but only a few minor anomalies found in trisomy 21 and in monosomy of proximal 21q, respectively.
我们报告了一名患有多种轻微异常且21号染色体异常重排的智力发育迟缓儿童。这条der(21)染色体有21p和近端21q的缺失,而21q的主要部分发生了重复,导致出现镜面对称外观,镜轴位于断点处。着丝粒仅在一个意外的远端位置表现为一个次级缢痕(具有G染色体的着丝粒指数),但用染色体特异性或所有人着丝粒α卫星DNA进行荧光原位杂交(FISH)均未显示交叉杂交。因此,这条标记染色体代表了“具有新着丝粒的非α卫星标记”的又一个例子。使用21号染色体上的多态性标记进行分子分析证实了21号染色体近端长臂有一个非常小的单体片段,此外,剩余远端片段为三体。尽管几乎整个21q臂为三体,但我们的患者没有典型的唐氏综合征表型,仅分别在21三体和近端21q单体中发现了一些轻微异常。