Delvaux V, Sciot R, Neuville B, Moerman P, Peeters M, Filez L, Van Beckevoort D, Ectors N, Geboes K
Department of Pathology, University Hospitals Leuven, Belgium.
Virchows Arch. 2000 Jul;437(1):90-4. doi: 10.1007/s004280000183.
A 67-year-old man presented with weight loss, intermittent severe abdominal pain and melaena. Initial radiology (including abdominal ultrasonography), gastroscopy and colonoscopy did not demonstrate any lesions that could explain the complaints. Three weeks later, upper gastrointestinal and small-bowel barium studies revealed two areas in the small intestine with an abnormal mucosal pattern. Explorative laparotomy revealed three tumoral lesions. Three partial enterectomies were performed. Gross examination showed centrally depressed dark reddish tumoral lesions extending from the mucosa throughout the full thickness of the bowel wall (diameter varying between 1.6 cm and 2.2 cm). The tumours, composed of large, plump, polygonal cells showing little architectural differentiation, were mainly situated in submucosa and muscularis propria. The growth pattern appeared rather solid. The epithelioid cells showed pronounced nuclear pleomorphism and atypia with central large nucleoli. There were several small blood vessels with occasional anaplastic endothelial cells. Immunohistochemical staining demonstrated an intense expression of CD 31, CD 34, factor VIII related antigen and keratin. This supported the diagnosis of an epithelioid angiosarcoma. The patient died 3 months after diagnosis. Tumours of the small intestine are very rare, and angiosarcomas of the small intestine are even more rare. Epithelioid variants have only been described in two patients and only one of these had a multifocal presentation. The prognosis is very poor. Because of the epithelioid growth pattern and the cytokeratin expression, these tumours may erroneously be diagnosed as a carcinoma.
一名67岁男性出现体重减轻、间歇性严重腹痛和黑便。最初的影像学检查(包括腹部超声)、胃镜和结肠镜检查均未发现可解释这些症状的病变。三周后,上消化道和小肠钡剂造影显示小肠有两个区域黏膜形态异常。剖腹探查发现三个肿瘤性病变,进行了三次部分肠切除术。大体检查显示中央凹陷的暗红色肿瘤性病变,从黏膜延伸至肠壁全层(直径在1.6厘米至2.2厘米之间)。肿瘤由大的、饱满的多边形细胞组成,结构分化不明显,主要位于黏膜下层和固有肌层。生长模式呈实性。上皮样细胞显示明显的核多形性和异型性,核仁大且位于中央。有几条小血管,偶尔可见间变的内皮细胞。免疫组化染色显示CD 31、CD 34、VIII因子相关抗原和角蛋白强烈表达。这支持上皮样血管肉瘤的诊断。患者在诊断后3个月死亡。小肠肿瘤非常罕见,小肠血管肉瘤更为罕见。上皮样变体仅在两名患者中被描述过,其中只有一名患者有多处病变。预后非常差。由于其上皮样生长模式和细胞角蛋白表达,这些肿瘤可能会被误诊为癌。