Rogers J G, Geho W B
J Bone Joint Surg Am. 1979 Sep;61(6A):909-14.
Fibrodysplasia ossificans progressiva in children can often be recognized at birth because of the presence of shortening of the great toe, characteristic hallux valgus, and short thumbs. The majority of patients have the onset of symptoms by the age of four years, but there is often a delay of many months before the diagnosis is made. Early recognition will allow protection of the child from injuries in which the damaged tissue will serve as a focus of calcification. Most patients with this condition are physically disabled. The site of onset and of greatest involvement is axial. Biopsy and surgery are best avoided. Use of EHDP (disodium ethane 1-hydroxy, 1-diphosphonate, or disodium etidronate) is not as yet of proved value in most patients. Data from this study support the concept that most cases of this lesion arise as dominant mutations.
儿童进行性骨化性纤维发育不良通常在出生时就能被识别,因为存在大脚趾缩短、典型的拇外翻和短拇指。大多数患者在四岁时开始出现症状,但在确诊之前往往会有长达数月的延迟。早期识别可以保护儿童免受损伤,因为受损组织会成为钙化的病灶。患有这种疾病的大多数患者身体残疾。发病部位和受累最严重的部位是躯干。最好避免活检和手术。在大多数患者中,使用依替膦酸二钠(1-羟基-1-乙烷二膦酸二钠或依替膦酸钠)尚未被证明有价值。这项研究的数据支持了这样一种观点,即这种病变的大多数病例是由显性突变引起的。