Grosso Salvatore, Mostardini Rosa, Venturi Carlo, Bracco Sandra, Casasco Alfredo, Berardi Rosario, Balestri Paolo
Department of Pediatrics, University of Siena, Siena, Italy.
Neurosurgery. 2002 Jan;50(1):204-7; discussion 207-8. doi: 10.1097/00006123-200201000-00031.
Torticollis is a symptom that can be related to different pathological mechanisms ranging from simple to life-threatening conditions. We report a child with recurrent torticollis caused by an intracranial dissecting vertebral artery aneurysm. This is a very rare condition in childhood, and it was resolved successfully with endovascular treatment.
The patient was a 10-year-old boy with a 4-year history of left recurrent torticollis, followed by hemiparesis, dysarthria, dysmetria, and tremor. Brain magnetic resonance imaging and digital angiography detected a dissecting aneurysm involving the fourth segment of the left vertebral artery.
The patient underwent endovascular treatment. Coil embolization, followed by histoacryl injection into the lesion, provided complete obliteration of the aneurysmal sac.
The patient's postoperative course was characterized by a dramatic disappearance of symptoms and signs within a few hours of the intervention. No relapses of symptoms occurred during a follow-up period of 18 months. This is the first report of a child in whom recurrent torticollis was related to a dissecting vertebral artery aneurysm. Although long-term results of vertebral artery coil embolization remain to be elucidated, the method seems reliable and effective in treatment of these vascular lesions in pediatric patients.
斜颈是一种症状,可与从简单到危及生命的不同病理机制相关。我们报告一名儿童,其复发性斜颈由颅内椎动脉夹层动脉瘤引起。这在儿童期是一种非常罕见的情况,通过血管内治疗成功解决。
患者为一名10岁男孩,有4年左侧复发性斜颈病史,随后出现偏瘫、构音障碍、辨距不良和震颤。脑部磁共振成像和数字血管造影检测到一个累及左侧椎动脉第四段的夹层动脉瘤。
患者接受了血管内治疗。先进行弹簧圈栓塞,然后向病变部位注射组织黏合剂,使动脉瘤囊完全闭塞。
患者术后病程的特点是在干预后数小时内症状和体征显著消失。在18个月的随访期内未出现症状复发。这是第一例复发性斜颈与椎动脉夹层动脉瘤相关的儿童病例报告。尽管椎动脉弹簧圈栓塞的长期结果仍有待阐明,但该方法在治疗小儿患者的这些血管病变方面似乎可靠且有效。