Schramm Vern L
Department of Biochemistry, Albert Einstein College of Medicine, 1300 Morris Park Avenue, Forch. 308, Bronx, NY 10461, USA.
Biochim Biophys Acta. 2002 Jul 18;1587(2-3):107-17. doi: 10.1016/s0925-4439(02)00073-x.
Newborns with a genetic deficiency of purine nucleoside phosphorylase (PNP) are normal, but exhibit a specific T-cell immunodeficiency during the first years of development. All other cell and organ systems remain functional. The biological significance of human PNP is degradation of deoxyguanosine, and apoptosis of T-cells occurs as a consequence of the accumulation of deoxyguanosine in the circulation, and dGTP in the cells. Control of T-cell proliferation is desirable in T-cell cancers, autoimmune diseases, and tissue transplant rejection. The search for powerful inhibitors of PNP as anti-T-cell agents has culminated in the immucillins. These inhibitors have been developed from knowledge of the transition state structure for the reactions catalyzed by PNP, and inhibit with picomolar dissociation constants. Immucillin-H (Imm-H) causes deoxyguanosine-dependent apoptosis of rapidly dividing human T-cells, but not other cell types. Human T-cell leukemia cells, and stimulated normal T-cells are both highly sensitive to the combination of Imm-H to block PNP and deoxyguanosine. Deoxyguanosine is the cytotoxin, and Imm-H alone has low toxicity. Single doses of Imm-H to mice cause accumulation of deoxyguanosine in the blood, and its administration prolongs the life of immunodeficient mice in a human T-cell tissue xenograft model. Immucillins are capable of providing complete control of in vivo PNP levels and hold promise for treatment of proliferative T-cell disorders.
嘌呤核苷磷酸化酶(PNP)基因缺陷的新生儿出生时正常,但在发育的最初几年会出现特定的T细胞免疫缺陷。所有其他细胞和器官系统仍保持功能。人PNP的生物学意义在于降解脱氧鸟苷,由于循环中脱氧鸟苷和细胞内dGTP的积累,会导致T细胞凋亡。在T细胞癌症、自身免疫性疾病和组织移植排斥反应中,控制T细胞增殖是很有必要的。寻找强大的PNP抑制剂作为抗T细胞药物的研究最终产生了免疫菌素。这些抑制剂是根据对PNP催化反应的过渡态结构的了解而开发的,其解离常数为皮摩尔级。免疫菌素-H(Imm-H)会导致快速分裂的人T细胞发生依赖脱氧鸟苷的凋亡,但对其他细胞类型无此作用。人T细胞白血病细胞和受刺激的正常T细胞对Imm-H阻断PNP和脱氧鸟苷的联合作用都高度敏感。脱氧鸟苷是细胞毒素,单独使用Imm-H毒性较低。给小鼠单次注射Imm-H会导致血液中脱氧鸟苷积累,在人T细胞组织异种移植模型中,给予Imm-H可延长免疫缺陷小鼠的寿命。免疫菌素能够完全控制体内PNP水平,有望用于治疗增殖性T细胞疾病。