Lee Chang-Woo, Bang Hoil, Oh Yeon-Gyun, Yun Hyang-Suk, Kim Jong-Duck, Coe Chang-Jun
Department of Pediatrics, Yonsei University College of Medicine, Institute for Handicapped Children, 134 Shinchon-dong, Seodaemun-gu, Seoul 120-752, Korea.
Yonsei Med J. 2003 Apr 30;44(2):331-5. doi: 10.3349/ymj.2003.44.2.331.
Neuronal ceroid lipofuscinosis, which is also known as Batten-Bielschowsky disease, is a group of neuro degenerative disorders, associated with various progressive symptoms including seizures, dementia, visual loss and cerebral atrophy. We experienced a case of late infantile neuronal ceroid lipofuscinosis in a 6-year-old boy who had progressive myoclonic seizures, ataxia, rapid psychomotor deterioration and visual loss. Photic stimulation at 2 to 5 Hz elicited a discrete spike and wave discharges in the occipital region on an electroencephalogram. Magnetic resonance imaging of the brain showed generalized cerebral and cerebellar atrophy. An electron microscopic examination of the skin revealed characteristic curvilinear inclusion bodies. An optic fundoscopy revealed a devastated retina and severe optic atrophy. We report this case with the brief review of related literature.
神经元蜡样脂褐质沉积症,也被称为巴滕-比尔绍斯基病,是一组神经退行性疾病,伴有各种进行性症状,包括癫痫发作、痴呆、视力丧失和脑萎缩。我们遇到一例6岁男孩的晚期婴儿型神经元蜡样脂褐质沉积症,该男孩有进行性肌阵挛性癫痫发作、共济失调、快速精神运动发育迟缓以及视力丧失。脑电图显示,2至5赫兹的光刺激在枕叶区域诱发离散的棘波和慢波放电。脑部磁共振成像显示大脑和小脑普遍萎缩。皮肤电子显微镜检查发现特征性的曲线包涵体。眼底镜检查显示视网膜严重受损和严重视神经萎缩。我们报告此病例并简要回顾相关文献。