Guan Na, Ding Jie, Zhang Jingjing, Yang Jiyun
Department of Pediatrics, Peking University First Hospital, Peking, China.
Pediatr Nephrol. 2003 Nov;18(11):1122-7. doi: 10.1007/s00467-003-1240-z. Epub 2003 Sep 5.
Recently, nephrin, podocin, alpha-actinin, and WT1, which are located at the slit diaphragm and expressed by the podocyte, were found to be causative in congenital/familial nephrotic syndrome (NS), but their role in acquired NS remains unclear. We studied their expression in NS with the aim of disclosing their possible role in the development of proteinuria. Immunofluorescence, confocal microscopy, and image analysis were used to study the expression and the distribution in 19 children with primary NS, 9 with isolated hematuria, and 9 controls. All the children with NS presented with heavy proteinuria and foot process effacement was identified by electron microscopy. No proteinuria and foot process effacement was seen in the group with hematuria. A dramatic decrease of podocin expression was found in NS (86.66+/-22.74) compared with control groups ( P=0.014). Furthermore, we also found the pattern of distribution of nephrin, podocin, and alpha-actinin changed in children with NS. In conclusion, a dramatic decrease of podocin expression and abnormal distribution of nephrin, podocin, and alpha-actinin were found in children with NS. No differences were found in children with isolated hematuria, suggesting involvement of these molecules in the development of proteinuria in primary NS.
最近,位于裂孔隔膜且由足细胞表达的nephrin、podocin、α -辅肌动蛋白和WT1被发现与先天性/家族性肾病综合征(NS)的发病有关,但它们在获得性NS中的作用仍不清楚。我们研究了它们在NS中的表达,旨在揭示它们在蛋白尿发生发展中的可能作用。采用免疫荧光、共聚焦显微镜和图像分析技术,对19例原发性NS患儿、9例孤立性血尿患儿及9例对照者进行了表达和分布研究。所有NS患儿均有大量蛋白尿,电镜检查发现足突消失。血尿组未见蛋白尿和足突消失。与对照组相比,NS组中podocin表达显著降低(86.66±22.74)(P = 0.014)。此外,我们还发现NS患儿中nephrin、podocin和α -辅肌动蛋白的分布模式发生了变化。总之,NS患儿中发现podocin表达显著降低,nephrin、podocin和α -辅肌动蛋白分布异常。孤立性血尿患儿未见差异,提示这些分子参与原发性NS蛋白尿的发生发展。