Lee J S, Tsai W Y, Tsai W S, Tsau Y K, Chen C H, Wang T R
Department of Pediatrics, National Taiwan University Hospital, Taipei, R.O.C.
J Formos Med Assoc. 1992 Jun;91(6):643-6.
Familial nephrogenic diabetes insipidus is a hereditary disorder, generally transmitted by sex-linked recessive genes with varying degrees of penetrance in females. The onset of this disorder occurs in infancy, usually characterized by unexplained fever, recurrent dehydration and failure to thrive. If left unrecognized, recurrent hyperosmolality and hypernatremia will lead to retarded growth and neurologic sequelae. Intracranial hemorrhage, consciousness disturbance and even mortality may occur in cases of acute dehydration episodes. We report on two families with nephrogenic diabetes insipidus, whose various symptoms and signs were studied to establish an accurate diagnosis. In pediatric practices, it is very important to recognize early those infants with obscure symptoms in order to preserve their psychomotor development and growth potential.
家族性肾性尿崩症是一种遗传性疾病,通常由X连锁隐性基因遗传,在女性中有不同程度的外显率。这种疾病在婴儿期发病,通常表现为不明原因的发热、反复脱水和生长发育迟缓。如果未被识别,反复的高渗血症和高钠血症将导致生长发育迟缓及神经后遗症。急性脱水发作时可能发生颅内出血、意识障碍甚至死亡。我们报告了两个患有肾性尿崩症的家族,对其各种症状和体征进行了研究以建立准确的诊断。在儿科临床中,早期识别那些症状不明显的婴儿非常重要,以便保护他们的精神运动发育和生长潜力。