Navon P, Yarom A, Davis E
Department of Pediatrics, Bikur-Cholim General Hospital, Jerusalem, Israel.
J Mal Vasc. 1992;17(4):273-6.
Raynaud's phenomenon, uncommon in childhood, often heralds connective tissue disorder. Since microvascular abnormalities can be detected at an early stage of the connective tissue disease, especially in scleroderma, a specific diagnosis can be made in patients presenting with Raynaud's phenomenon alone or Raynaud's phenomenon associated with symptoms suggestive of connective tissue disease. Raynaud's phenomenon was studied in 11 consecutive children, 10 girls and 1 boy, ages 6 to 15. One child had a definite diagnosis of cutaneous polyarteritis nodosa. In 6 others connective tissue disease was suspected: 4 had arthritis, 2 has telangiectasia, leg ulcers and antinuclear antibodies. Of the remaining 4, one had hemiplegia and 3 Raynaud's phenomenon only. Oscillometry of the radial artery was reduced in 7 of 9. Decreased capillary resistance was found in 2 of 6, while abrupt thinning in conjunctival vessels was seen in 3 of 7. On nailfold capillaroscopy, reduced vascularity was noted in 5 of 11, dilated capillaries in 4 of 11, tortuousity in 2 of 11, capillary thinning in 1 of 11, capillary spasm in 1 of 11 and normal pattern in 3 of 11. Two patients presenting with Raynaud's phenomenon were found to have "scleroderma-like pattern" on nailfold capillaroscopy. One of them died 2 years later of cardiopulmonary sclerosis, and another developed esophageal stricture and Barrett's esophagus. Neither has sclerodermatous skin. In childhood Raynaud's phenomenon, nailfold capillaroscopy is a non-invasive examination enabling early diagnosis of "systemic scleroderma sine scleroderma".
雷诺现象在儿童期并不常见,常预示着结缔组织病。由于在结缔组织病的早期阶段就能检测到微血管异常,尤其是在硬皮病中,因此对于仅表现为雷诺现象或伴有提示结缔组织病症状的雷诺现象的患者,可以做出明确诊断。对11名年龄在6至15岁的连续儿童进行了雷诺现象研究,其中10名女孩和1名男孩。1名儿童被明确诊断为皮肤型结节性多动脉炎。另外6名怀疑患有结缔组织病:4名有关节炎,2名有毛细血管扩张、腿部溃疡和抗核抗体。其余4名中,1名有偏瘫,3名仅有雷诺现象。9名中的7名桡动脉示波测量值降低。6名中的2名发现毛细血管阻力降低,7名中的3名结膜血管出现突然变细。在甲襞毛细血管镜检查中,11名中的5名血管减少,11名中的4名毛细血管扩张,11名中的2名迂曲,11名中的1名毛细血管变细,11名中的1名毛细血管痉挛,11名中的3名正常。两名出现雷诺现象的患者在甲襞毛细血管镜检查中发现有“硬皮病样模式”。其中1名在2年后死于心肺硬化,另1名出现食管狭窄和巴雷特食管。两人均无硬皮病样皮肤。在儿童期雷诺现象中,甲襞毛细血管镜检查是一种非侵入性检查,能够早期诊断“无硬皮病的系统性硬皮病”。