Isaac Sherif, Athanasou Nicholas A, Pike Michael, Burge Peter D
Nuffield Orthopaedic Centre, Oxford, United Kingdom.
J Child Neurol. 2004 Jan;19(1):71-5. doi: 10.1177/08830738040190010711.
Localized hypertrophic neuropathy, also termed intraneural perineurioma, is a rare disorder of unknown etiology that produces a slowly progressive painless focal lesion of a peripheral nerve. It is characterized histologically by concentric whorls ("onion bulbs") of epithelial membrane antigen-reactive, S-100 protein-negative perineurial cells surrounding nerve fibers. We report a radial nerve palsy in a child aged 2 years in whom the diagnosis of localized hypertrophic neuropathy was made by biopsy. Resection of the affected nerve segment and sural nerve grafting produced no useful recovery after 3 years, probably because of the long duration of denervation. When this mononeuropathy presents in early childhood, uncertainty over the time of onset can lead to difficulty in distinguishing this potentially treatable lesion from congenital and other causes of nerve palsy.
局限性肥厚性神经病,也称为神经内神经束膜瘤,是一种病因不明的罕见疾病,可在外周神经产生缓慢进展的无痛性局灶性病变。其组织学特征是围绕神经纤维的上皮膜抗原反应性、S-100蛋白阴性的神经束膜细胞呈同心性涡旋(“洋葱球”)。我们报告了一名2岁儿童的桡神经麻痹,通过活检确诊为局限性肥厚性神经病。切除受影响的神经节段并进行腓肠神经移植,3年后未获得有效恢复,可能是因为失神经支配时间过长。当这种单神经病在幼儿期出现时,发病时间的不确定性可能导致难以将这种潜在可治疗的病变与先天性及其他原因引起的神经麻痹区分开来。