Suppr超能文献

迟发性皮肤卟啉症与遗传性血色素沉着症的关联。

Association of porphyria cutanea tarda with hereditary hemochromatosis.

作者信息

Mehrany Khosrow, Drage Lisa A, Brandhagen David J, Pittelkow Mark R

机构信息

Department of Dermatology, Mayo Clinic, Rochester, MN 55905, USA.

出版信息

J Am Acad Dermatol. 2004 Aug;51(2):205-11. doi: 10.1016/j.jaad.2003.08.015.

Abstract

BACKGROUND

An increased frequency of hereditary hemochromatosis gene mutations occurs in patients with porphyria cutanea tarda. Polymerase chain reaction analysis of peripheral blood for hemochromatosis gene (HFE) mutations is available for clinical use. Early detection and treatment of hereditary hemochromatosis limit disease progression and improve life expectancy.

OBJECTIVE

We present 8 patients with porphyria cutanea tarda subsequently found to have hereditary hemochromatosis or mutations in the HFE gene.

METHODS

Retrospective review of patients in whom both porphyria cutanea tarda and hereditary hemochromatosis or HFE gene mutations were diagnosed between 1976 and 2000.

RESULTS

Eight patients with porphyria cutanea tarda (6 males, 2 females; age range, 4-60 years; mean age at diagnosis of porphyria cutanea tarda, 42 years) were subsequently found to have hepatic iron overload or HFE gene mutations. Two patients had liver biopsy findings compatible with homozygous hereditary hemochromatosis. In the other 6 patients, HFE gene analysis revealed 3 homozygous C282Y, 1 compound heterozygous C282Y/H63D, and 2 heterozygous C282Y mutations. Seven patients (88%) had no specific signs or symptoms of hereditary hemochromatosis at diagnosis. In 5 patients (63%), the diagnosis of hereditary hemochromatosis or HFE gene mutation was initially suspected by the dermatologist.

CONCLUSION

Porphyria cutanea tarda can be an important cutaneous marker for patients with mutations of the HFE gene. HFE gene analysis should be done in patients who present with porphyria cutanea tarda. The dermatologist may play a key role in the early diagnosis of subclinical hereditary hemochromatosis in patients who present with porphyria cutanea tarda.

摘要

背景

迟发性皮肤卟啉病患者中遗传性血色素沉着症基因突变的频率增加。外周血血色素沉着症基因(HFE)突变的聚合酶链反应分析可用于临床。遗传性血色素沉着症的早期检测和治疗可限制疾病进展并提高预期寿命。

目的

我们报告8例迟发性皮肤卟啉病患者,随后发现他们患有遗传性血色素沉着症或HFE基因突变。

方法

回顾性分析1976年至2000年间诊断为迟发性皮肤卟啉病和遗传性血色素沉着症或HFE基因突变的患者。

结果

8例迟发性皮肤卟啉病患者(6例男性,2例女性;年龄范围4至60岁;迟发性皮肤卟啉病诊断时的平均年龄为42岁)随后被发现有肝铁过载或HFE基因突变。2例患者的肝活检结果符合纯合子遗传性血色素沉着症。在其他6例患者中,HFE基因分析显示3例纯合子C282Y、1例复合杂合子C282Y/H63D和2例杂合子C282Y突变。7例患者(88%)在诊断时无遗传性血色素沉着症的特异性体征或症状。5例患者(63%)中,皮肤科医生最初怀疑为遗传性血色素沉着症或HFE基因突变。

结论

迟发性皮肤卟啉病可能是HFE基因突变患者的重要皮肤标志物。出现迟发性皮肤卟啉病的患者应进行HFE基因分析。皮肤科医生在出现迟发性皮肤卟啉病的患者亚临床遗传性血色素沉着症的早期诊断中可能起关键作用。

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验