Acar Aydin, Eryilmaz Adil, Gocer Celil, Akmansu Halit, Korkmaz Hakan
Otorhinolaryngology Department, Ankara Numune Hospital, Cemal Gursel Cad. No. 44/A, Kurtuluş, Ankara, Turkey.
Int J Pediatr Otorhinolaryngol. 2004 Dec;68(12):1557-61. doi: 10.1016/j.ijporl.2004.07.012.
Lipoid proteinosis is a rare autosomal recessive disorder characterized by intercellular deposition of an amorphous hyaline material. It mainly involves skin and mucosal membranes of upper aerodigestive tract as well as central nervous system, lung, lymph nodes and striated muscles. Etiology and pathogenesis are unknown. Infantile hoarseness is a common presenting feature of the disease due to infiltration of larynx. In two-thirds of the cases, voice changes are present at birth or in early infancy as the first manifestation. We present four patients with lipoid proteinosis involving skin, oropharynx and larynx.
类脂蛋白沉积症是一种罕见的常染色体隐性疾病,其特征为无定形透明质物质在细胞间沉积。它主要累及上呼吸道消化道的皮肤和黏膜,以及中枢神经系统、肺、淋巴结和横纹肌。病因和发病机制尚不清楚。由于喉部浸润,婴儿期声音嘶哑是该疾病常见的表现特征。在三分之二的病例中,出生时或婴儿早期就出现声音改变作为首发表现。我们报告了4例累及皮肤、口咽和喉部的类脂蛋白沉积症患者。