Yavarian Majid, Karimi Mehran, Zorai Amine, Harteveld Cornelis L, Giordano Piero C
Hemoglobinopathies Laboratory, Department of Human and Clinical Genetics, Leiden University Medical Center, AL Leiden, The Netherlands.
Hemoglobin. 2005;29(1):43-50.
Although alpha0-thalassemia (thal) defects are not very frequent in the Iranian population, Hb H disease does occur in the country. We have analyzed the alpha gene cluster of 13 patients showing the presence of Hb H to establish the molecular background of this disease in southwest Iran (Shiraz and Hormozgan provinces). Using gap-polymerase chain reaction (gap-PCR) and direct DNA sequencing we have found the --MED-I deletion, the polyadenylation signal (poly A) mutations alphaT-Saudi alpha and alphaT-Turkish alpha and Hb Constant Spring (Hb CS) in association with the common -alpha3.7 deletion. This study has revealed that: 1) at least six genotypes are responsible for Hb H disease in the area: .-alpha3.7/ --MED-I; -alpha3.7/alphaT-Saudi alpha; alphaT-Saudi alpha/alphaT-Saudi alpha; alphaCSalpha/--MED-I; --MED-I/alphaT-Turkish alpha; and the atypical forms of Hb H disease -alpha3.7/alphaCSalpha. 2) The molecular background of Hb H disease in the southwest area of Iran is more similar to the Mediterranean type than to the Southeast Asian. 3) Hb Bart's hydrops fetalis syndrome and mild, intermediate or severe postnatal Hb H disease conditions can be expected, but at a relatively low incidence. 4) The diagnostic flowchart for patients with microcytic hypochromic anemia should include iron deficiency, beta-thal, alpha+- and alpha0-thal analyses.
尽管α0地中海贫血(地贫)缺陷在伊朗人群中并不常见,但该国确实存在Hb H病。我们分析了13例出现Hb H的患者的α基因簇,以确定伊朗西南部(设拉子和霍尔木兹甘省)这种疾病的分子背景。通过缺口聚合酶链反应(gap-PCR)和直接DNA测序,我们发现了--MED-I缺失、多聚腺苷酸化信号(poly A)突变αT-沙特α和αT-土耳其α以及与常见的-α3.7缺失相关的Hb Constant Spring(Hb CS)。这项研究表明:1)该地区至少有六种基因型导致Hb H病:.-α3.7/--MED-I;-α3.7/αT-沙特α;αT-沙特α/αT-沙特α;αCSα/--MED-I;--MED-I/αT-土耳其α;以及Hb H病的非典型形式-α3.7/αCSα。2)伊朗西南部地区Hb H病的分子背景与地中海型比与东南亚型更相似。3)可以预期会出现Hb Bart水肿胎儿综合征以及轻度、中度或重度产后Hb H病情况,但发病率相对较低。4)小细胞低色素性贫血患者的诊断流程图应包括缺铁、β地贫、α+和α0地贫分析。