Karmous-Benailly Houda, Tabet Anne-Claude, Thaly Adeline, Dupuy Olivier, Huten Yolène, Luton Dominique, Baumann Clarisse, Delezoide Anne-Lise
Service de Biologie du Développement, Hôpital Robert Debré, Paris, France.
Prenat Diagn. 2005 Mar;25(3):193-7. doi: 10.1002/pd.1102.
Trisomy of the short arm of chromosome 4 is a well-known syndrome, and several observations have been made in the last 30 years. Herein, we report a new observation of trisomy 4p in a fetus with a semi-lobar holoprosencephaly (HPE), dysmorphic features and multiple malformations. The diagnosis of HPE was made, at 33 weeks' gestation, on the fetus of a healthy G1P0 woman. Amniocentesis was performed for chromosome analysis and additional material was found on a chromosome 22. The couple elected to terminate the pregnancy and fetal examination was realized. Conventional and molecular cytogenetic studies were performed on the fetus and the parents, which showed that the additional material found on one chromosome 22 corresponded to the short arm of chromosome 4 and therefore led us to establish a diagnosis of trisomy 4p inherited from the malsegregation of a paternal translocation t(4;22)(q12;q11.1). The etiology of HPE is very heterogeneous; it includes non-genetic factors such as maternal diabetes and genetic causes. HPE cases have been described in association with many chromosomal anomalies, trisomy 13 being the most frequent. However, to our knowledge, HPE has never been previously reported in association with a trisomy involving solely the short arm of chromosome 4.
4号染色体短臂三体是一种广为人知的综合征,在过去30年里已有多项观察报道。在此,我们报告了1例患有半侧脑叶全前脑畸形(HPE)、畸形特征和多种畸形的胎儿4号染色体短臂三体的新观察结果。在妊娠33周时,对一名健康的初产妇(G1P0)的胎儿做出了HPE的诊断。进行了羊水穿刺以进行染色体分析,在22号染色体上发现了额外的物质。这对夫妇选择终止妊娠并对胎儿进行了检查。对胎儿及其父母进行了常规和分子细胞遗传学研究,结果显示在一条22号染色体上发现的额外物质对应于4号染色体的短臂,因此我们诊断该胎儿为因父源t(4;22)(q12;q11.1)易位错误分离而遗传的4号染色体短臂三体。HPE的病因非常异质,包括母体糖尿病等非遗传因素和遗传原因。HPE病例已被描述与许多染色体异常有关,其中13号染色体三体最为常见。然而,据我们所知,此前从未有过HPE与仅涉及4号染色体短臂的三体相关的报道。