Tulinius Már, Moslemi Ali-Reza, Darin Niklas, Holme Elisabeth, Oldfors Anders
The Queen Silvia Children's Hospital, S-416 85 Göteborg, Sweden.
Neuromuscul Disord. 2005 Jun;15(6):412-5. doi: 10.1016/j.nmd.2005.03.010.
We describe the clinical, morphological and genetic findings in two siblings with the myopathic form of mitochondrial DNA depletion syndrome (MIM 251880). Sequencing of the thymidine kinase-2 gene revealed two heterozygous missense mutations, a C-->T mutation at nucleotide 191 resulting in a change of threonine to methionine at residue 64 in exon 3, and a C-->T mutation at nucleotide 547 resulting in an arginine to tryptophan amino acid change at residue 183 in exon 8. Both mutations changed highly conserved residues in the gene and neither one has been described previously. This report extends the phenotypic expression of mutations in the thymidine kinase-2 gene.
我们描述了两名患有肌病型线粒体DNA耗竭综合征(MIM 251880)的同胞的临床、形态学和遗传学发现。胸苷激酶-2基因测序显示两个杂合错义突变,核苷酸191处的C→T突变导致外显子3中第64位残基的苏氨酸变为甲硫氨酸,核苷酸547处的C→T突变导致外显子8中第183位残基的精氨酸变为色氨酸。这两个突变均改变了该基因中高度保守的残基,且之前均未被描述过。本报告扩展了胸苷激酶-2基因突变的表型表达。