Morgans Catherine W, Ren Gaoying, Akileswaran Lakshmi
Neurological Sciences Institute, Oregon Health and Science University, Beaverton, 97006, USA.
Eur J Neurosci. 2006 Mar;23(5):1163-71. doi: 10.1111/j.1460-9568.2006.04647.x.
Complete X-linked congenital stationary night blindness (CSNB1) is a hereditary visual disease characterized by abnormalities in both the dark- and light-adapted electroretinogram, consistent with a defect in synaptic transmission between photoreceptors and ON-bipolar cells. The gene responsible for CSNB1, NYX, encodes a novel, leucine-rich repeat protein, nyctalopin. Consistent with its predicted glycosylphosphatidylinositol linkage, we show that recombinant nyctalopin is targeted to the extracellular cell surface in transfected HEK293 cells. Within the retina, strong nyctalopin immunoreactivity is present in the outer plexiform layer, the site of the photoreceptor to bipolar cell synapses. Double labelling of nyctalopin and known synaptic proteins in the outer plexiform layer indicate that nyctalopin is associated with the ribbon synapses of both rod and cone terminals. In the inner plexiform layer, nyctalopin immunoreactivity is associated with rod bipolar cell terminals. Our findings support a role for nyctalopin in synaptic transmission and/or synapse formation at ribbon synapses in the retina.
完全性X连锁先天性静止性夜盲(CSNB1)是一种遗传性视觉疾病,其特征为暗适应和明适应视网膜电图均异常,这与光感受器和ON双极细胞之间的突触传递缺陷一致。导致CSNB1的基因NYX编码一种新型富含亮氨酸重复序列蛋白——夜盲蛋白。与其预测的糖基磷脂酰肌醇连接方式相符,我们发现重组夜盲蛋白在转染的HEK293细胞中定位于细胞外表面。在视网膜内,外网状层存在强烈的夜盲蛋白免疫反应性,外网状层是光感受器与双极细胞突触所在部位。外网状层夜盲蛋白与已知突触蛋白的双重标记表明,夜盲蛋白与视杆和视锥终末的带状突触相关。在内网状层,夜盲蛋白免疫反应性与视杆双极细胞终末相关。我们的研究结果支持夜盲蛋白在视网膜带状突触的突触传递和/或突触形成中发挥作用。