Wu Hui-Chung, Lin Lung-Huang, Tsai Li-Ping, Huang Cheng-Hung, Hung Kun-Long, Liao Hung-Tsai
Department of Pediatrics, Cathay General Hospital- Sijhih, No. 2, Lane 59, Jiancheng Rd., Sijhih City, Taipei 221, Taiwan.
Acta Paediatr Taiwan. 2006 May-Jun;47(3):139-41.
Pallister-Killian Syndrome (PKS) is a rare sporadic congenital anomaly disorder, characterized by multiple congenital anomalies, especially craniofacial dysmorphism. It is also associated with mental retardation, seizure, skin pigmentation, and visceral malformations such as congenital diaphragmatic hernia, congenital heart defect, anorectal anomalies, and genital malformation. This syndrome usually presents with tissue-limited mosaicism of supernumerary 12p isochromosome i (12p). Moreover, diagnosis of Pallister-Killian Syndrome (PKS) is difficult because the ratio of abnormal to normal karyotyping is much lower in peripheral lymphocytes than in skin fibroblasts. We report the first case in Taiwan, who has tetrasomy 12p mosaic in peripheral lymphocytes.
帕利斯特-基利安综合征(PKS)是一种罕见的散发性先天性异常疾病,其特征为多种先天性异常,尤其是颅面部畸形。它还与智力发育迟缓、癫痫、皮肤色素沉着以及内脏畸形有关,如先天性膈疝、先天性心脏缺陷、肛门直肠畸形和生殖器畸形。该综合征通常表现为额外的12号等臂染色体i(12p)的组织局限性嵌合体。此外,帕利斯特-基利安综合征(PKS)的诊断较为困难,因为外周淋巴细胞中异常核型与正常核型的比例远低于皮肤成纤维细胞。我们报告了台湾首例外周淋巴细胞中存在12号染色体四体嵌合体的病例。